Vetter U, Maierhofer B, Müller M, Lang D, Teller W M, Brenner R, Frohneberg D, Wörsdörfer O
Kinderklinik, Universität Ulm, Federal Republic of Germany.
Eur J Pediatr. 1989 Dec;149(3):184-7. doi: 10.1007/BF01958277.
We examined 58 children aged 1-16 years with various forms of osteogenesis imperfecta (OI). Congenital cardiac malformations were diagnosed in 4 children (valvular aortic stenosis, 2 with atrial septal defect II, Fallot Tetralogy). Two additional children developed holosystolic mitral valve prolapse and regurgitation. Children suffering from a severe clinical course (type III according to the Sillence classification) showed aortic root dilatation (28%) and increased septal (40%) and posterior left ventricular wall thickening (68%) on initial evaluation. All three parameters were significantly correlated to body surface area. Kidney stones and renal papillary calcifications were detected in 4 children. Cardiovascular abnormalities and nephrolithiasis may be important extraskeletal manifestations of childhood OI.
我们检查了58名年龄在1至16岁之间、患有各种类型成骨不全症(OI)的儿童。4名儿童被诊断出患有先天性心脏畸形(瓣膜性主动脉狭窄、2例继发孔型房间隔缺损、法洛四联症)。另外两名儿童出现全收缩期二尖瓣脱垂和反流。患有严重临床病程(根据席伦斯分类为III型)的儿童在初次评估时显示主动脉根部扩张(28%),室间隔增厚(40%)以及左心室后壁增厚(68%)。所有这三个参数均与体表面积显著相关。4名儿童检测出肾结石和肾乳头钙化。心血管异常和肾结石可能是儿童OI重要的骨骼外表现。