Wang Junmei, Liu Zhaoxia, Fang Jingyi, Du Jiang, Cui Yun, Xu Li, Li Guilin
Department of Neuropathology, Beijing Neurosurgical Institute, China National Clinical Research Center for Neurological Diseases (NCRC-ND), Brain Tumor Center, Beijing Institute for Brain Disorders, Beijing Key Brain Tumor Laboratory, Capital Medical University, No. 6 Tiantan Xili, Dongcheng, Beijing, 100050, China.
Brain Tumor Pathol. 2016 Oct;33(4):261-266. doi: 10.1007/s10014-016-0267-3. Epub 2016 Jun 15.
Atypical teratoid/rhabdoid tumor (AT/RT) is a rare, highly malignant tumor of the central nervous system (CNS) that typically occurs during infancy. These tumors exhibit morphologic heterogeneity and differentiate along multiple lineages, thus posing a diagnostic challenge. Here, we present two cases of AT/RT with a primitive neuroectodermal component and histological pattern resembling an embryonal tumor with multilayered rosettes (ETMR), a rare but distinctive embryonal entity with different therapeutic implications. Patient 1, a 23-month-old girl, presented with a history of gait unsteadiness and headache; cranial computed tomography (CT) identified a mass in the pineal and third ventricular regions. Patient 2, a 26-month-old girl, presented with headache and vomiting; CT revealed a mass in the posterior third ventricle. Both patients were treated via gross total tumor resection. Although histologically, AT/RT cases variably comprise primitive neuroectodermal, mesenchymal, and classic rhabdoid cells, the most striking feature of both cases was the presence of multilayered rosettes with a few Homer Wright rosettes and occasional primitive neuroepithelial tubes in focal primitive component areas. Immunohistochemistry revealed considerable heterogeneity within the tumors. We further present our findings in the context of the relevant literature.
非典型畸胎样/横纹肌样肿瘤(AT/RT)是一种罕见的、高度恶性的中枢神经系统(CNS)肿瘤,通常发生于婴儿期。这些肿瘤表现出形态学异质性,并沿多个谱系分化,因此带来了诊断挑战。在此,我们报告两例具有原始神经外胚层成分且组织学模式类似于伴有多层菊形团的胚胎性肿瘤(ETMR)的AT/RT病例,ETMR是一种罕见但独特的胚胎性实体,具有不同的治疗意义。病例1为一名23个月大的女孩,有步态不稳和头痛病史;头颅计算机断层扫描(CT)发现松果体区和第三脑室区域有一个肿块。病例2为一名26个月大的女孩,有头痛和呕吐症状;CT显示第三脑室后部有一个肿块。两名患者均接受了肿瘤全切手术。尽管在组织学上,AT/RT病例可变地由原始神经外胚层、间充质和经典横纹肌样细胞组成,但这两例最显著的特征是在局灶性原始成分区域存在多层菊形团,伴有一些霍纳·赖特菊形团和偶尔的原始神经上皮管。免疫组织化学显示肿瘤内部存在相当大的异质性。我们还结合相关文献介绍了我们的研究结果。