Sánchez Torres G, Roldán Conesa D
Instituto Nacional de Cardiología Ignacio Chávez, México, D.F.
Arch Inst Cardiol Mex. 1989 Mar-Apr;59(2):125-31.
We studied a case of a patent left ductus arteriosus, with a left aortic arch connected to a right descending aorta without an aortic circumflex (retroesophageal) segment. We believe this is the first world-published example of this--so far--hypothetical anomaly, included in Kirkling and Edwards classification of vascular rings. The case was a 27-year-old deaf-mute female patient with a patent left ductus arteriosus, with important left to right shunt and moderate pulmonary arterial hypertension who underwent a successful closing surgical procedure. In the aortographic study a left (normal) aortic arch was seen, which after giving off a large left ductus arteriosus, crossed to the right and connected to a right descending aorta. In the upper part of the thorax the esophagus and trachea were displaced to the right by the left aortic arch. The esophagus in the middle and the upper inferior parts of the thorax was also displaced to the right by the descending right aortic segment. Complete vascular ring was not evident. The case--although without clinical importance--reinforces the pathogenic concept of the Rathke diagram of a complete double aortic primitive arch originating the pulmonary and supraaortic vascular structures which are formed by the obliteration or disappearance of particular segments of the structure. This knowledge explains the embryogenesis of these complex anomalies. Our case is believed to be formed by the very early disappearance of a frontal portion of the primitive left dorsal aorta.
我们研究了一例动脉导管未闭病例,其左主动脉弓与右位降主动脉相连,无主动脉弓环(食管后)段。我们认为这是世界上首次发表的此类迄今为止仍属假设的异常病例,该病例被纳入Kirkling和Edwards血管环分类中。该病例为一名27岁的聋哑女性患者,患有动脉导管未闭,存在明显的左向右分流及中度肺动脉高压,接受了成功的闭合手术。在主动脉造影研究中,可见一个左(正常)主动脉弓,发出一个粗大的动脉导管未闭后,跨过中线与右位降主动脉相连。在胸部上部,食管和气管被左主动脉弓向右推移。胸部中下部的食管也被右位降主动脉段向右推移。完整的血管环不明显。该病例——尽管无临床意义——强化了Rathke图中关于由原始双主动脉弓形成肺血管和主动脉上血管结构的致病概念,这些结构是由该结构特定节段的闭塞或消失形成的。这一知识解释了这些复杂异常的胚胎发生过程。我们认为该病例是由原始左背主动脉前部极早期消失形成的。