Grinfeld Jacob, Godfrey Anna L
Department of Haematology, Cambridge University Hospitals NHS Foundation Trust, Hills Rd, Cambridge CB2 0QQ, UK.
Blood Rev. 2017 May;31(3):101-118. doi: 10.1016/j.blre.2016.11.001. Epub 2016 Nov 15.
The JAK2V617F mutation accounts for the vast majority of patients with polycythaemia vera (PV) and around half of those with other Philadelphia-negative myeloproliferative neoplasms. Since its discovery in 2005, numerous insights have been gained into the pathways by which JAK2V617F causes myeloproliferation, including activation of JAK-STAT signalling but also through other canonical and non-canonical pathways. A variety of mechanisms explain how this one mutation can be associated with distinct clinical disorders, demonstrating how constitutional and acquired factors may interact in the presence of a single mutation to determine disease phenotype. Important biological questions remain unanswered in PV, in particular how JAK2V617F affects stem cell function and what mechanisms drive myelofibrotic and leukaemic transformation. Whilst current management is largely centred on prevention of cardiovascular events, future therapies must aim to target the JAK2-mutant clone, to reverse the underlying marrow pathology and to address the risk of transformation events.
JAK2V617F突变在绝大多数真性红细胞增多症(PV)患者中存在,在其他费城染色体阴性的骨髓增殖性肿瘤患者中约占一半。自2005年发现该突变以来,人们对JAK2V617F导致骨髓增殖的途径有了诸多认识,包括JAK-STAT信号通路的激活,但也涉及其他经典和非经典途径。多种机制解释了这一单一突变如何与不同的临床疾病相关联,表明在单一突变存在的情况下,体质因素和后天因素可能相互作用以决定疾病表型。PV中仍有一些重要的生物学问题未得到解答,特别是JAK2V617F如何影响干细胞功能以及哪些机制驱动骨髓纤维化和白血病转化。虽然目前的治疗主要集中在预防心血管事件,但未来的治疗必须旨在靶向JAK2突变克隆,逆转潜在的骨髓病理状态,并应对转化事件的风险。