Simpson Ewan A, Jaring Matthew R F, Andronikou Savvas
*Department of Paediatric Radiology, Bristol Royal Hospital for Children, University Hospitals Bristol NHS Foundation Trust †CRIC Bristol, University of Bristol, Bristol, UK.
J Pediatr Hematol Oncol. 2017 Jul;39(5):e300-e301. doi: 10.1097/MPH.0000000000000763.
Protein-losing enteropathy due to massive mesenteric lymphadenopathy is a rare complication of Gaucher disease which is generally refractory to treatment with enzyme replacement and substrate reduction therapies. It is postulated that lymph nodes may act as a "sanctuary site" into which these treatments cannot penetrate. We present the case of a male child with Gaucher disease who developed massive mesenteric lymph nodes despite otherwise successful treatment with enzyme replacement therapy, and subsequently developed protein-losing enteropathy. The sonographic and magnetic resonance appearances of this complication are shown. Large volume lymphadenopathy inevitably provokes concern about the possibility of malignancy, but in a patient with Gaucher disease-particularly with significant ascites and clinical features of protein-losing enteropathy-this rare complication should be considered.
由于大量肠系膜淋巴结病导致的蛋白丢失性肠病是戈谢病的一种罕见并发症,通常对酶替代疗法和底物减少疗法难治。据推测,淋巴结可能充当这些治疗无法渗透的“庇护所”。我们报告一例患有戈谢病的男童病例,尽管酶替代疗法在其他方面治疗成功,但他仍出现了大量肠系膜淋巴结,随后发展为蛋白丢失性肠病。展示了该并发症的超声和磁共振表现。大量淋巴结病不可避免地引发对恶性肿瘤可能性的担忧,但对于戈谢病患者,尤其是伴有大量腹水和蛋白丢失性肠病临床特征的患者,应考虑这种罕见并发症。