University Children's Hospital, Münster, Germany.
Cincinnati Children's Hospital Medical Center, Cincinnati, Ohio.
Arthritis Rheumatol. 2017 Jul;69(7):1480-1494. doi: 10.1002/art.40099. Epub 2017 Jun 12.
Systemic-onset juvenile idiopathic arthritis (JIA) is speculated to follow a biphasic course, with an initial systemic disease phase driven by innate immune mechanisms and interleukin-1β (IL-1β) as a key cytokine and a second chronic arthritic phase that may be dominated by adaptive immunity and cytokines such as IL-17A. Although a recent mouse model points to a critical role of IL-17-expressing γ/δ T cells in disease pathology, in humans, both the prevalence of IL-17 and the role of IL-17-producing cells are still unclear.
Serum samples from systemic JIA patients and healthy pediatric controls were analyzed for the levels of IL-17A and related cytokines. Whole blood samples were studied for cellular expression of IL-17 and interferon-γ (IFNγ). CD4+ and γ/δ T cells isolated from the patients and controls were assayed for cytokine secretion in different culture systems.
IL-17A was prevalent in sera from patients with active systemic JIA, while both ex vivo and in vitro experiments revealed that γ/δ T cells overexpressed this cytokine. This was not seen with CD4+ T cells, which expressed strikingly low levels of IFNγ. Therapeutic IL-1 blockade was associated with partial normalization of both cytokine expression phenotypes. Furthermore, culturing healthy donor γ/δ T cells in serum from systemic JIA patients or in medium spiked with IL-1β, IL-18, and S100A12 induced IL-17 overexpression at levels similar to those observed in the patients' cells.
A systemic JIA cytokine environment may prime γ/δ T cells in particular for IL-17A overexpression. Thus, our observations in systemic JIA patients strongly support a pathophysiologic role of these cells, as proposed by the recent murine model.
全身性幼年特发性关节炎(JIA)被推测存在双相病程,初始的全身性疾病阶段由先天免疫机制和白细胞介素-1β(IL-1β)驱动,后者是关键细胞因子,而第二个慢性关节炎阶段可能由适应性免疫和细胞因子如 IL-17A 主导。尽管最近的小鼠模型表明表达 IL-17 的γ/δ T 细胞在疾病病理中起关键作用,但在人类中,IL-17 的流行程度和产生 IL-17 的细胞的作用仍不清楚。
分析全身性 JIA 患者和健康儿科对照者的血清样本中 IL-17A 和相关细胞因子的水平。研究全血样本中 IL-17 和干扰素-γ(IFNγ)的细胞表达。从患者和对照者中分离 CD4+和γ/δ T 细胞,并在不同的培养系统中检测细胞因子的分泌。
活动期全身性 JIA 患者的血清中存在 IL-17A,而体外和体内实验均表明 γ/δ T 细胞过度表达这种细胞因子。CD4+T 细胞则没有这种情况,其 IFNγ 的表达水平明显较低。IL-1 阻断治疗与两种细胞因子表达表型的部分正常化相关。此外,在血清中培养健康供体γ/δ T 细胞从全身性 JIA 患者或在含有 IL-1β、IL-18 和 S100A12 的培养基中培养,会诱导类似患者细胞中观察到的 IL-17 过度表达。
全身性 JIA 的细胞因子环境可能特别促使 γ/δ T 细胞过度表达 IL-17A。因此,我们在全身性 JIA 患者中的观察结果强烈支持这些细胞的病理生理作用,正如最近的小鼠模型所提出的那样。