Department of Psychiatry and Neuropsychology, School for Mental Health and Neuroscience, Maastricht University, Maastricht, The Netherlands.
Genmab, Utrecht, The Netherlands.
Sci Rep. 2017 Apr 20;7(1):992. doi: 10.1038/s41598-017-01019-5.
Autoantibodies against ion channels are the cause of numerous neurologic autoimmune disorders. Frequently, such pathogenic autoantibodies have a restricted epitope-specificity. In such cases, competing antibody formats devoid of pathogenic effector functions (blocker antibodies) have the potential to treat disease by displacing autoantibodies from their target. Here, we have used a model of the neuromuscular autoimmune disease myasthenia gravis in rhesus monkeys (Macaca mulatta) to test the therapeutic potential of a new blocker antibody: MG was induced by passive transfer of pathogenic acetylcholine receptor-specific monoclonal antibody IgG1-637. The effect of the blocker antibody (IgG4Δhinge-637, the hinge-deleted IgG4 version of IgG1-637) was assessed using decrement measurements and single-fiber electromyography. Three daily doses of 1.7 mg/kg IgG1-637 (cumulative dose 5 mg/kg) induced impairment of neuromuscular transmission, as demonstrated by significantly increased jitter, synaptic transmission failures (blockings) and a decrease in the amplitude of the compound muscle action potentials during repeated stimulations (decrement), without showing overt symptoms of muscle weakness. Treatment with three daily doses of 10 mg/kg IgG4Δhinge-637 significantly reduced the IgG1-637-induced increase in jitter, blockings and decrement. Together, these results represent proof-of principle data for therapy of acetylcholine receptor-myasthenia gravis with a monovalent antibody format that blocks binding of pathogenic autoantibodies.
自身抗体针对离子通道是许多神经自身免疫性疾病的原因。通常,这种致病性自身抗体具有有限的表位特异性。在这种情况下,缺乏致病性效应功能的竞争抗体形式(阻断抗体)有可能通过将自身抗体从其靶标上置换来治疗疾病。在这里,我们使用恒河猴(Macaca mulatta)的神经肌肉自身免疫性疾病重症肌无力模型来测试新型阻断抗体的治疗潜力:通过被动转移致病性乙酰胆碱受体特异性单克隆抗体 IgG1-637 诱导 MG。使用递减测量和单纤维肌电图评估阻断抗体(IgG4Δhinge-637,IgG1-637 的铰链缺失 IgG4 版本)的效果。三次每日剂量 1.7mg/kg IgG1-637(累积剂量 5mg/kg)导致神经肌肉传递受损,表现为明显增加的抖动、突触传递失败(阻滞)和在重复刺激时复合肌肉动作电位幅度降低(递减),而没有出现明显的肌肉无力症状。用三次每日剂量 10mg/kg IgG4Δhinge-637 治疗可显著降低 IgG1-637 诱导的抖动、阻滞和递减增加。这些结果共同代表了使用单价抗体形式阻断致病性自身抗体结合来治疗乙酰胆碱受体重症肌无力的原理验证数据。