Nishimura Shunji, Hashimoto Kazuhiko, Tan Akihiro, Yagyu Yukinobu, Akagi Masao
Department of Orthopedic Surgery, Kindai University Faculty of Medicine, Osakasayama, Osaka 589-8511, Japan.
Department of Orthopedic Surgery, Sakibana Hospital, Izumi, Osaka 594-1105, Japan.
Mol Clin Oncol. 2017 Mar;6(3):307-310. doi: 10.3892/mco.2017.1137. Epub 2017 Jan 23.
Giant cell tumor of bone (GCTB) is commonly treated with surgery; however, surgery of GCTB in the sacrum may be challenging due to the associated risk. A conservative approach may be selective arterial embolization or zoledronic acid (ZOL) treatment; however, there are currently no studies investigating the efficacy of combining these two treatments. Denosumab may also be used; however, to the best of our knowledge, there are no reports of a stepwise approach for the use of all three treatments in a single patient. We herein present such a case. A 32-year-old woman diagnosed with sacral GCTB was treated with selective arterial embolization for 3 months. No improvement was observed, and monthly infusions of ZOL were added (administered 2 weeks after each arterial embolization treatment). Ten months after the initiation of ZOL, there was still no improvement. The therapy was changed to denosumab 120 mg, injected subcutaneously once a month. By the third dose, the buttock pain had decreased and the patient became ambulatory. At 5 and 10 months, computed tomography scans revealed bone sclerosis gradually appearing around the sacrum. By 1 year, needle biopsy detected no neoplastic cells. At that point, the patient discontinued treatment, as there was hepatic function impairment due to a history of hepatitis B. Despite treatment discontinuation, the patient exhibited no further symptoms, there were no signs of progression on radiography, and surgery was not required. Our patient experienced treatment failure with selective arterial embolization. The combination of ZOL with selective arterial embolization also did not improve the patient's condition. Denosumab was found to be superior to both treatments, achieving tumor remission. The patient remains symptom- and disease-free. Further studies are required, but our results suggest that patients with unresectable GCTB who fail to respond to selective arterial embolization may benefit from denosumab treatment, but not from combination therapy with selective arterial embolization and ZOL.
骨巨细胞瘤(GCTB)通常采用手术治疗;然而,由于相关风险,骶骨GCTB的手术可能具有挑战性。保守治疗方法可能是选择性动脉栓塞或唑来膦酸(ZOL)治疗;然而,目前尚无研究调查这两种治疗方法联合使用的疗效。地诺单抗也可使用;然而,据我们所知,尚无关于在单一患者中逐步使用这三种治疗方法的报道。我们在此报告这样一个病例。一名32岁被诊断为骶骨GCTB的女性接受了3个月的选择性动脉栓塞治疗。未观察到改善,随后添加了每月一次的ZOL输注(在每次动脉栓塞治疗后2周给药)。开始使用ZOL 10个月后,仍无改善。治疗改为每月皮下注射一次120mg地诺单抗。到第三剂时,臀部疼痛减轻,患者能够行走。在5个月和10个月时,计算机断层扫描显示骶骨周围逐渐出现骨质硬化。到1年时,穿刺活检未检测到肿瘤细胞。此时,由于有乙型肝炎病史导致肝功能损害,患者停止治疗。尽管停止治疗,但患者未出现进一步症状,影像学检查无进展迹象,也无需手术。我们的患者选择性动脉栓塞治疗失败。ZOL与选择性动脉栓塞联合使用也未改善患者病情。发现地诺单抗优于这两种治疗方法,实现了肿瘤缓解。患者仍无症状且无疾病。需要进一步研究,但我们的结果表明,对选择性动脉栓塞无反应的不可切除GCTB患者可能从地诺单抗治疗中获益,但不能从选择性动脉栓塞与ZOL的联合治疗中获益。