Guo Jianman, Grovola Michael R, Xie Hong, Coggins Grace E, Duggan Patrick, Hasan Rukhsana, Huang Jiale, Lin Danny W, Song Claire, Witek Gabriela M, Berritt Simon, Schultz David C, Field Jeffrey
Department of Systems Pharmacology and Translational Therapeutics, Perelman School of Medicine, University of PennsylvaniaPhiladelphia, PA 19104, USA.
Institute of Clinical Pharmacology, Qilu Hospital of Shandong UniversityJinan 250012, Shandong, P. R. China.
Am J Cancer Res. 2017 Apr 1;7(4):923-934. eCollection 2017.
Patients with Neurofibromatosis type 1 (NF1) and Neurofibromatosis type 2 (NF2) are predisposed to tumors of the nervous system. NF1 patients predominantly develop neurofibromas, and Malignant Peripheral Nerve Sheath Tumors (MPNST) while NF2 patients develop schwannomas and meningiomas. Here we quantified the drug sensitivities of NF1 and NF2 tumor cell lines in a high throughput platform. The platform contained a comprehensive collection of inhibitors of MEK, RAF, RAS, farnesyl transferase, PAK and ERK, representative drugs against many other cancer pathways including Wnt, Hedgehog, p53, EGF, HDAC, as well as classical cytotoxic agents recommended for treating MPNST, such as doxorubicin and etoposide. We profiled seven NF1-associated MPNST cell lines (ST88-14, ST88-3, 90-8, sNF02.2, T265, S462TY, SNF96.2), one sporadic MPNST cell line (STS26), one schwannoma from a NF2 patient (HEI193), one NF2-deficient malignant meningioma (KT21-MG-Luc5D), one mouse NF2 schwannoma (SC4) and one sporadic rat schwannoma (RT4-67 or RT4). NF1 cells were primarily distinguished from NF2 cells and the sporadic MPNST cell line by their sensitivity to MEK and ERK inhibitors, and to a smaller extent their sensitivity to BH3 mimetics and farnesyl transferase inhibitors. The platform was highly successful in predicting the effects of clinical trials for Neurofibromas.
1型神经纤维瘤病(NF1)和2型神经纤维瘤病(NF2)患者易患神经系统肿瘤。NF1患者主要发生神经纤维瘤和恶性外周神经鞘膜瘤(MPNST),而NF2患者则发生神经鞘瘤和脑膜瘤。在此,我们在一个高通量平台上对NF1和NF2肿瘤细胞系的药物敏感性进行了量化。该平台包含了MEK、RAF、RAS、法尼基转移酶、PAK和ERK抑制剂的全面集合,以及针对许多其他癌症通路的代表性药物,包括Wnt、Hedgehog、p53、EGF、HDAC,还有推荐用于治疗MPNST的经典细胞毒性药物,如阿霉素和依托泊苷。我们分析了7种与NF1相关的MPNST细胞系(ST88 - 14、ST88 - 3、90 - 8、sNF02.2、T265、S462TY、SNF96.2)、1种散发性MPNST细胞系(STS26)、1例来自NF2患者的神经鞘瘤(HEI193)、1例NF2缺陷型恶性脑膜瘤(KT21 - MG - Luc5D)、1例小鼠NF2神经鞘瘤(SC4)和1例散发性大鼠神经鞘瘤(RT4 - 67或RT4)。NF1细胞与NF2细胞及散发性MPNST细胞系的主要区别在于它们对MEK和ERK抑制剂的敏感性,以及在较小程度上对BH3模拟物和法尼基转移酶抑制剂的敏感性。该平台在预测神经纤维瘤临床试验效果方面非常成功。