Cabrera-Salcedo Catalina, Kumar Priya, Hwa Vivian, Dauber Andrew
Cincinnati Center for Growth Disorders, Division of Endocrinology, Cincinnati Children's Hospital Medical Center. Cincinnati, OH, USA.
Pediatr Endocrinol Rev. 2017 Mar;14(3):289-297. doi: 10.17458/per.vol14.2017.SKHD.imageandrelatedundergrowth.
CDKN1C is a cyclin-dependent kinase Inhibitor and negative regulator of cellular proliferation. Recently, gain-of-function mutations in the PCNA domain of CDKN1C have been reported as the genetic basis of various growth-retarded syndromes including IMAGe syndrome, Russell Silver syndrome as well as a novel undergrowth syndrome that additionally exhibited early adulthood onset diabetes. This review summarizes the key clinical features and the molecular advances that have contributed to our understanding of this complex phenotypic spectrum.
CDKN1C是一种细胞周期蛋白依赖性激酶抑制剂,也是细胞增殖的负调节因子。最近,有报道称CDKN1C的PCNA结构域中的功能获得性突变是包括IMAGe综合征、罗素-西尔弗综合征以及一种额外表现为成年早期发病糖尿病的新型发育迟缓综合征等各种生长发育迟缓综合征的遗传基础。这篇综述总结了关键的临床特征以及有助于我们理解这一复杂表型谱的分子进展。