Finsterer Josef, Scorza Fulvio Alexandre
Neurological Department, Municipal Hospital Rudolfstiftung, A-1030 Vienna, Austria.
Paulista de Medicina School, Federal University of São Paulo, Primeiro Andar CEP, São Paulo 04039-032, SP, Brazil.
Biomed Rep. 2017 May;6(5):487-494. doi: 10.3892/br.2017.892. Epub 2017 Apr 12.
The aim of the present review was to summarize and discuss previous findings concerning renal manifestations of primary mitochondrial disorders (MIDs). A literature review was performed using frequently used databases. The study identified that primary MIDs frequently present as mitochondrial multiorgan disorder syndrome (MIMODS) at onset or in the later course of the MID. Occasionally, the kidneys are affected in MIDs. Renal manifestations of MIDs include renal insufficiency, nephrolithiasis, nephrotic syndrome, renal cysts, renal tubular acidosis, Bartter-like syndrome, Fanconi syndrome, focal segmental glomerulosclerosis, tubulointerstitial nephritis, nephrocalcinosis, and benign or malign neoplasms. Among the syndromic MIDs, renal involvement has been most frequently reported in patients with mitochondrial encephalomyopathy, lactic acidosis, and stroke-like episodes syndrome, Kearns-Sayre syndrome, Leigh syndrome and mitochondrial depletion syndromes. Only in single cases was renal involvement also reported in chronic progressive external ophthalmoplegia, Pearson syndrome, Leber's hereditary optic neuropathy, coenzyme-Q deficiency, X-linked sideroblastic anemia and ataxia, myopathy, lactic acidosis, and sideroblastic anemia, pyruvate dehydrogenase deficiency, growth retardation, aminoaciduria, cholestasis, iron overload, lactacidosis, and early death, and hyperuricemia, pulmonary hypertension, renal failure in infancy and alkalosis syndrome. The present study proposes that the frequency of renal involvement in MIDs is probably underestimated. Diagnosis of renal involvement follows general guidelines and treatment is symptomatic. Thus, renal manifestations of primary MIDs require recognition and appropriate management, as they determine the outcome of MID patients.
本综述的目的是总结和讨论先前关于原发性线粒体疾病(MIDs)肾脏表现的研究结果。使用常用数据库进行了文献综述。该研究发现,原发性MIDs在发病时或病程后期常表现为线粒体多器官功能障碍综合征(MIMODS)。偶尔,肾脏也会受到MIDs的影响。MIDs的肾脏表现包括肾功能不全、肾结石、肾病综合征、肾囊肿、肾小管酸中毒、巴特综合征样综合征、范科尼综合征、局灶节段性肾小球硬化、肾小管间质性肾炎、肾钙质沉着症以及良性或恶性肿瘤。在综合征性MIDs中,线粒体脑肌病、乳酸酸中毒和卒中样发作综合征、凯-赛综合征、 Leigh综合征和线粒体耗竭综合征患者的肾脏受累情况报道最为频繁。仅在个别病例中,慢性进行性外眼肌麻痹、皮尔逊综合征、Leber遗传性视神经病变、辅酶Q缺乏症、X连锁铁粒幼细胞贫血伴共济失调、肌病、乳酸酸中毒和铁粒幼细胞贫血、丙酮酸脱氢酶缺乏症、生长发育迟缓、氨基酸尿症、胆汁淤积、铁过载、乳酸酸中毒和早期死亡,以及高尿酸血症、肺动脉高压、婴儿期肾衰竭和碱中毒综合征患者中也有肾脏受累的报道。本研究提出,MIDs肾脏受累的频率可能被低估了。肾脏受累的诊断遵循一般指南,治疗以对症治疗为主。因此,原发性MIDs的肾脏表现需要得到认识和适当管理,因为它们决定了MID患者的预后。