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眶尖囊肿:功能性鼻内镜鼻窦手术后压迫性视神经病变的罕见原因。

Orbital apex cyst: a rare cause of compressive optic neuropathy post-functional endoscopic sinus surgery.

作者信息

Koh Yi Ni, Ho Shu Fen, Pathma Letchumanan, Singh Harvinder, Zunaina Embong

机构信息

Department of Ophthalmology, School of Medical Sciences, Universiti Sains Malaysia, Kubang Kerian, Kelantan, Malaysia.

Department of Ophthalmology.

出版信息

Int Med Case Rep J. 2017 Jul 28;10:263-269. doi: 10.2147/IMCRJ.S124524. eCollection 2017.

DOI:10.2147/IMCRJ.S124524
PMID:28814902
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC5546777/
Abstract

There are various causes that can lead to compressive optic neuropathy. We present here orbital apex cyst as an unusual cause of compressive optic neuropathy in a 49-year-old male. He presented with 2 weeks painless loss of vision in the left eye with left-sided headache. He had had left functional endoscopic sinus surgery for left nasal polyps 4 years earlier. Magnetic resonance imaging of brain and orbit revealed a left discrete orbital nodule, possibly orbital cyst or mucocele, which was compressing on the left optic nerve. Left eye vision improved markedly from hand movement to 6/36 pinhole 6/18 after initiation of intravenous dexamethasone. A subsequent endoscopic endonasal left optic nerve decompression found the orbital nodule lesion to be an orbital cyst. Marsupialization was performed instead of excision, as the cyst ruptured intraoperatively. Postoperative vision improved to 6/7.5 with normal optic nerve function postoperatively. Possible cause of orbital apex cyst is discussed.

摘要

有多种病因可导致压迫性视神经病变。我们在此报告一例49岁男性因眶尖囊肿导致压迫性视神经病变的罕见病例。患者因左侧头痛伴左眼无痛性视力丧失2周就诊。4年前他曾因左侧鼻息肉接受过左侧功能性内镜鼻窦手术。脑部和眼眶的磁共振成像显示左侧有一个孤立的眶内结节,可能是眼眶囊肿或黏液囊肿,压迫左侧视神经。静脉注射地塞米松后,左眼视力从手动明显提高到针孔视力6/36,矫正后6/18。随后的内镜下经鼻左侧视神经减压术发现眶内结节病变为眼眶囊肿。由于囊肿在术中破裂,故行袋形缝合术而非切除术。术后视力提高到6/7.5,术后视神经功能正常。文中讨论了眶尖囊肿的可能病因。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/8a83/5546777/b4f4bfcd40b3/imcrj-10-263Fig4.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/8a83/5546777/375383c1e781/imcrj-10-263Fig1.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/8a83/5546777/6c31859e79b3/imcrj-10-263Fig2.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/8a83/5546777/28ff825f0634/imcrj-10-263Fig3.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/8a83/5546777/b4f4bfcd40b3/imcrj-10-263Fig4.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/8a83/5546777/375383c1e781/imcrj-10-263Fig1.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/8a83/5546777/6c31859e79b3/imcrj-10-263Fig2.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/8a83/5546777/28ff825f0634/imcrj-10-263Fig3.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/8a83/5546777/b4f4bfcd40b3/imcrj-10-263Fig4.jpg

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Respiratory epithelial cysts of the orbit.眼眶呼吸上皮囊肿
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Orbital epidermoid cysts: a diagnosis to consider.眼眶表皮样囊肿:需考虑的一种诊断。
J Ophthalmol. 2014;2014:508425. doi: 10.1155/2014/508425. Epub 2014 Sep 8.
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A suprasellar meningioma simulating atypical retrobulbar optic neuritis.一例模拟非典型球后视神经炎的鞍上脑膜瘤
J Chin Med Assoc. 2003 Nov;66(11):689-92.
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Differential diagnosis of intracranial lesions with high signal on T1 or low signal on T2-weighted MRI.T1加权磁共振成像(MRI)上呈高信号或T2加权MRI上呈低信号的颅内病变的鉴别诊断。
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Atypical features prompting neuroimaging in acute optic neuropathy in adults.成人急性视神经病变中提示进行神经影像学检查的非典型特征。
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