Department of Environmental Health and Center for Environmental Genetics.
Department of Internal Medicine Cardiology Division, University of Cincinnati College of Medicine, Cincinnati, Ohio 45267.
Toxicol Sci. 2017 Nov 1;160(1):74-82. doi: 10.1093/toxsci/kfx164.
Epidemiological studies in humans and research in vertebrates indicates that developmental exposure to 2,3,7,8-tetrachlorodibenzo-p-dioxin (TCDD), a ubiquitous and biopersistent environmental toxicant, is associated with incidence of early congenital heart disease in the embryo and later in the adult. TCDD-mediated toxicity depends on the aryl hydrocarbon receptor (AHR) but the role of the TCDD-activated AHR in cardiac function is not well-defined. To characterize the mechanisms responsible for AHR-mediated disruption of heart function, we generated several mouse strains with cardiomyocyte-specific Ahr gene knockout. Here, we report results on one of these strains in which the Ahr gene was deleted by cre recombinase regulated by the promoter of the cardiomyocyte-specific Nkx2.5 gene. We crossed mice with loxP-targeted Ahrfx/fx alleles with Nkx2.5+/cre mice bearing a "knock-in" cre recombinase gene integrated into one of the Nkx2.5 alleles. In these mice, loss of one Nkx2.5 allele is associated with disrupted cardiac development. In males, Nkx2.5 hemizygosity resulted in cardiac haploinsufficiency characterized by hypertrophy, dilated cardiomyopathy, and impaired ejection fraction. Ahr ablation protected Nkx2.5+/cre haploinsufficient males from cardiac dysfunction while inducing a significant increase in body weight. These effects were absent or largely blunted in females. Starting at 3 months of age, mice were exposed by oral gavage to 1 μg/kg/week of TCDD or control vehicle for an additional 2 months. TCDD exposure restored cardiac physiology in aging males, appearing to compensate for the heart dysfunction caused by Nkx2.5 hemizygosity. Our findings underscore the conclusion that deletion of the Ahr gene in cardiomyocytes protects males from heart dysfunction due to NKX2.5 haploinsufficiency.
人类流行病学研究和脊椎动物研究表明,发育过程中暴露于 2,3,7,8-四氯二苯并对二恶英(TCDD)这种普遍存在且具有生物持久性的环境毒物与胚胎期和成年期早期先天性心脏病的发病率有关。TCDD 介导的毒性取决于芳烃受体(AHR),但 TCDD 激活的 AHR 在心脏功能中的作用尚不清楚。为了阐明导致 AHR 介导的心脏功能障碍的机制,我们生成了几种心肌细胞特异性 Ahr 基因敲除的小鼠品系。在这里,我们报告了其中一种品系的结果,其中 Ahr 基因通过受心肌细胞特异性 Nkx2.5 基因启动子调控的 cre 重组酶被删除。我们将带有loxP 靶向 Ahrfx/fx 等位基因的小鼠与携带整合到一个 Nkx2.5 等位基因中的“敲入” cre 重组酶基因的 Nkx2.5+/cre 小鼠进行杂交。在这些小鼠中,一个 Nkx2.5 等位基因的缺失与心脏发育异常有关。在雄性中,Nkx2.5 半合子导致心脏单倍不足,表现为心肌肥厚、扩张型心肌病和射血分数受损。Ahr 缺失可保护 Nkx2.5+/cre 半合子不足的雄性免受心脏功能障碍,同时导致体重显著增加。而这些效应在雌性中不存在或基本减弱。从 3 个月大开始,通过口服灌胃给予小鼠每周 1μg/kg 的 TCDD 或对照载体,持续 2 个月。TCDD 暴露恢复了衰老雄性的心脏生理学,似乎补偿了 Nkx2.5 半合子不足引起的心脏功能障碍。我们的研究结果强调了这样一个结论,即心肌细胞中 Ahr 基因的缺失可保护雄性免受 Nkx2.5 单倍不足引起的心脏功能障碍。