Department of Medical Genetics, Iuliu Haţieganu University of Medicine and Pharmacy, Cluj-Napoca, Romania.
Department of Genetics, Ion Chiricuţă Cancer Institute, Cluj-Napoca, Romania.
Am J Hematol. 2018 Jan;93(1):100-106. doi: 10.1002/ajh.24946. Epub 2017 Nov 10.
Polycythemia vera (PV), essential thrombocythemia (ET) and primary myelofibrosis (PMF) are classical myeloproliferative neoplasms (MPN), characterized by specific somatic mutations in JAK2, CALR or MPL genes. JAK2 46/1 and TERT rs2736100 polymorphisms are known to significantly predispose to MPN. This study aimed to establish the additional contribution of the recently described MECOM rs2201862, HBS1L-MYB rs9376092 and THRB-RARB rs4858647 polymorphisms to the occurrence of MPN. These three polymorphisms, along with JAK2 46/1 and TERT rs2736100 were genotyped in 939 MPN patients (454 with ET, 337 with PV and 148 with PMF) and 483 controls. MECOM rs2201862 associated significantly with each MPN entity, except for ET, and with all major molecular sub-types, especially those CALR-mutated (OR = 1.4; 95% CI = 1.1-1.8; P-value = .005). HBS1L-MYB rs9376092 associated only with JAK2 V617F-mutated ET (OR = 1.4; 95% CI = 1.1-1.7; P-value = .003). THRB-RARB rs4858647 had a weak association with PMF only (OR = 1.5; 95% CI = 1-2.1; P-value = .04). Surprisingly, JAK2 46/1 haplotype was associated significantly not only with JAK2 V617F-mutated MPN, but also with CALR-mutated MPN (OR = 1.4; 95% CI = 1.1-1.8; P-value = .01). TERT rs2736100 was associated equally strong with all MPN, regardless of phenotype or molecular sub-type. In conclusion, JAK2 46/1, TERT rs2736100 and MECOM rs2201862 are the chief predisposing polymorphisms to MPN.
真性红细胞增多症(PV)、特发性血小板增多症(ET)和原发性骨髓纤维化(PMF)是经典的骨髓增殖性肿瘤(MPN),其特征是 JAK2、CALR 或 MPL 基因的特异性体细胞突变。JAK2 46/1 和 TERT rs2736100 多态性已知显著增加 MPN 的易感性。本研究旨在确定最近描述的 MECOM rs2201862、HBS1L-MYB rs9376092 和 THRB-RARB rs4858647 多态性对 MPN 发生的额外贡献。这三种多态性与 JAK2 46/1 和 TERT rs2736100 一起在 939 名 MPN 患者(454 名 ET、337 名 PV 和 148 名 PMF)和 483 名对照中进行了基因分型。MECOM rs2201862 与除 ET 以外的每种 MPN 实体以及所有主要分子亚型显著相关,尤其是 CALR 突变型(OR=1.4;95%CI=1.1-1.8;P 值=0.005)。HBS1L-MYB rs9376092 仅与 JAK2 V617F 突变型 ET 相关(OR=1.4;95%CI=1.1-1.7;P 值=0.003)。THRB-RARB rs4858647 仅与 PMF 弱相关(OR=1.5;95%CI=1-2.1;P 值=0.04)。令人惊讶的是,JAK2 46/1 单倍型不仅与 JAK2 V617F 突变型 MPN 显著相关,而且与 CALR 突变型 MPN 相关(OR=1.4;95%CI=1.1-1.8;P 值=0.01)。TERT rs2736100 与所有 MPN 同样强烈相关,无论表型或分子亚型如何。总之,JAK2 46/1、TERT rs2736100 和 MECOM rs2201862 是 MPN 的主要易感性多态性。