Pakdel Farzad, Pirmarzdashti Niloofar, Soltani Sasan, Nozarian Zohreh, Asadi Amoli Fahimeh, Kassaee Abolfazl
Ophthalmic Plastic & Reconstructive Surgery Department, Farabi Hospital, Tehran University of Medical Sciences, Eye Research Center, Farabi Hospital, and Pathology Department, Farabi Hospital, Tehran University of Medical Sciences, Tehran, Iran.
Ophthalmic Plast Reconstr Surg. 2018 Mar/Apr;34(2):e41-e43. doi: 10.1097/IOP.0000000000001005.
The authors aim to report a 68-year-old patient presenting with acute swelling and redness of orbital area diagnosed initially as orbital cellulitis. Surgical excision was decided based on clinical and imaging findings with the diagnosis of pleomorphic adenoma of the lacrimal gland. Lacrimal gland pleomorphic adenoma usually presents with painless gradual swelling of upper eyelid. In an exceptionally rare circumstance, this case showed acute orbital inflammation, and imaging findings of orbital inflammation mostly focused around the cystic space of the lacrimal gland tumor. Histologic evaluation confirmed a ruptured cystic space of pleomorphic adenoma with foreign body-type inflammatory reaction. The authors propose spontaneous rupture of cystic space in the lacrimal gland pleomorphic adenoma as underlying mechanism for acute presentation of this tumor. Imaging and clinical characteristics and also prognostic implication of this phenomenon are discussed.
作者旨在报告一名68岁患者,其眼眶区域出现急性肿胀和发红,最初被诊断为眼眶蜂窝织炎。根据临床和影像学检查结果决定进行手术切除,诊断为泪腺多形性腺瘤。泪腺多形性腺瘤通常表现为上睑无痛性逐渐肿胀。在一种极为罕见的情况下,该病例表现为急性眼眶炎症,眼眶炎症的影像学表现主要集中在泪腺肿瘤的囊性区域周围。组织学评估证实多形性腺瘤的囊性区域破裂并伴有异物型炎症反应。作者提出泪腺多形性腺瘤囊性区域的自发破裂是该肿瘤急性表现的潜在机制。本文讨论了这种现象的影像学和临床特征以及预后意义。