Holsten Till, Tsiakas Konstantinos, Kordes Uwe, Bison Brigitte, Pietsch Torsten, Rutkowski Stefan, Santer René, Schüller Ulrich
Department of Pediatric Hematology and Oncology, University Medical Center Hamburg-Eppendorf, Hamburg, Germany.
Institute of Neuropathology, University Medical Center Hamburg-Eppendorf, Hamburg, Germany.
Childs Nerv Syst. 2018 Mar;34(3):581-584. doi: 10.1007/s00381-017-3666-9. Epub 2017 Nov 22.
Glycogen storage disease (GSD) 0a is a rare congenital metabolic disease with symptoms in infancy and childhood caused by biallelic GYS2 germline variants. A predisposition to cancer has not been described yet. We report here a boy with GSD 0a, who developed a malignant brain tumor at the age of 4.5 years. The tumor was classified as a group 3 medulloblastoma, and the patient died from cancer 27 months after initial tumor diagnosis. This case appears interesting as group 3 medulloblastoma is so far not known to arise in hereditary syndromes and the biology of sporadic group 3 medulloblastoma is largely unknown.
糖原贮积病(GSD)0a是一种罕见的先天性代谢疾病,由双等位基因GYS2种系变异引起,在婴儿期和儿童期出现症状。尚未有患癌倾向的相关描述。我们在此报告一名患有GSD 0a的男孩,他在4.5岁时患上了恶性脑肿瘤。该肿瘤被归类为3组髓母细胞瘤,患者在初次肿瘤诊断后27个月死于癌症。这个病例显得很有意思,因为目前尚不知道3组髓母细胞瘤会出现在遗传性综合征中,而且散发性3组髓母细胞瘤的生物学特性在很大程度上也不清楚。