Department of Internal Medicine, CHU de Caen, Caen, France.
Department of Immunology, CHU de Caen, Caen, France.
PLoS One. 2018 Apr 5;13(4):e0195680. doi: 10.1371/journal.pone.0195680. eCollection 2018.
Recent data suggest the existence of a complement alternative pathway activation in the pathogenesis of antineutrophilic cytoplasmic antibody (ANCA)-associated vasculitis (AAV), a condition that remains poorly understood. This study aims to assess the clinical characteristics and outcomes of granulomatosis with polyangiitis (GPA) and microscopic polyangiitis (MPA) patients with regard to their plasma complement levels at diagnosis. A retrospective monocentric study carried out at Caen University Hospital led to the identification of proteinase-3- or myeloperoxidase-ANCA-positive GPA and MPA patients from January 2000 to June 2016 and from September 2011 to June 2016, respectively. All patients with available C3 and C4 levels at diagnosis were included. Patients were categorized in the hypocomplementemia group if their C3 and/or C4 levels at diagnosis were below the lower limit of the normal range. Among the 76 AAV patients (43 GPA, 33 MPA), 4 (5%) had hypocomplementemia, and the 72 remaining patients exhibited normal plasma complement levels. All 4 hypocomplementemia patients had renal involvement. Hypocomplementemia was followed in 1 patient whose post-treatment complement level normalized within 1 month. Among all clinical and ANCA specificity, including relapse-free survival (p = 0.093), only overall and renal survival rates were significantly lower in the hypocomplementemia group (p = 0.0011 and p<0.001, respectively). Hypocomplementemia with low C3 and/or C4 levels at GPA or MPA diagnosis may be responsible for worse survival and renal prognosis. These results argue for larger and prospective studies to better determine the epidemiology of the disease and to assess complement-targeting therapy in these patients.
最近的数据表明,在抗中性粒细胞胞浆抗体(ANCA)相关性血管炎(AAV)的发病机制中存在补体替代途径的激活,而这种情况仍然知之甚少。本研究旨在评估在诊断时血浆补体水平方面,肉芽肿性多血管炎(GPA)和显微镜下多血管炎(MPA)患者的临床特征和结局。在卡昂大学医院进行的一项回顾性单中心研究,鉴定了 2000 年 1 月至 2016 年 6 月间蛋白酶 3 或髓过氧化物酶-ANCA 阳性 GPA 和 MPA 患者,以及 2011 年 9 月至 2016 年 6 月间的相同患者。所有患者均有诊断时的 C3 和 C4 水平。如果患者在诊断时的 C3 和/或 C4 水平低于正常范围的下限,则将其归为低补体血症组。在 76 例 AAV 患者(43 例 GPA,33 例 MPA)中,4 例(5%)有低补体血症,其余 72 例患者的血浆补体水平正常。所有 4 例低补体血症患者均有肾脏受累。对 1 例患者进行了低补体血症随访,其治疗后补体水平在 1 个月内恢复正常。在所有临床和 ANCA 特异性中,包括无复发存活率(p = 0.093),只有低补体血症组的总存活率和肾脏存活率明显较低(p = 0.0011 和 p<0.001)。在 GPA 或 MPA 诊断时出现低 C3 和/或 C4 水平的低补体血症可能与较差的生存和肾脏预后有关。这些结果表明需要进行更大规模的前瞻性研究,以更好地确定疾病的流行病学,并评估这些患者的补体靶向治疗。