Kerkeni Yosra, Louati Hela, Hamzaoui Mourad
Department of Pediatric Surgery "A", Children Hospital "Bechir Hamza" of Tunis, Tunisia Université de Tunis El Manar, Faculté de Médecine de Tunis, Tunis, Tunisia.
Department of Radiology, Children Hospital "Bechir Hamza" of Tunis, Tunisia Université de Tunis El Manar, Faculté de Médecine de Tunis, Tunis, Tunisia.
Korean J Pediatr. 2018 Apr;61(4):132-134. doi: 10.3345/kjp.2018.61.4.132. Epub 2018 Apr 23.
We report a unique case of intestinal duplication detected on posterior reversible encephalopathy syndrome (PRES) in a 13-year-old girl. She was admitted to the pediatric Emergency Department because of generalized seizures. Radiological assessment revealed a large, well-defined, thick-walled cystic lesion in the mid abdomen, suggestive of duplication cyst associated to a PRES. Exploration confirmed the diagnosis of ileal duplication cyst, and the mass was resected. The postoperative course was uneventful. Both hypertension and neurological dysfunction resolved after the mass resection. A followup brain magnetic resonance imaging was performed 9 months later and showed complete resolution of the cerebellar changes. Although extrinsic compression of the retroperitoneal structures has not been reported in the literature as a complication of duplication cyst, we strongly believe that this is the most logical and plausible hypothesis that would explain the pathogenesis of PRES in our patient.
我们报告了一例独特的病例,一名13岁女孩在后部可逆性脑病综合征(PRES)中被检测出肠道重复畸形。她因全身性癫痫发作被收治入儿科急诊科。影像学评估显示中腹部有一个大的、边界清晰的、厚壁囊性病变,提示与PRES相关的重复囊肿。探查证实为回肠重复囊肿诊断,肿物被切除。术后过程顺利。肿物切除后高血压和神经功能障碍均得到缓解。9个月后进行了随访脑磁共振成像,显示小脑改变完全消退。尽管文献中未报道腹膜后结构的外在压迫是重复囊肿的并发症,但我们坚信这是解释我们患者PRES发病机制最合理且可信的假设。