Ma J, Ming C, Lou F, Wang M L, Lin K, Zeng W J, Li Z C, Liu X F, Zhang T S
Department of Otorhinolaryngology Head and Neck Surgery, Kunming Children's Hospital; Head and Neck Disease Treatment Center, Kunming 650228, China.
Zhonghua Er Bi Yan Hou Tou Jing Wai Ke Za Zhi. 2018 May 7;53(5):381-384. doi: 10.3760/cma.j.issn.1673-0860.2018.05.010.
To discuss the misdiagnosis of pyriform sinus fistula and to better understand this kind of illness. The analysis was based on twenty-eight patients with congenital pyriform sinus fistula aged from 11 months to 14 years, with the median age of 5 years, and who were surgically treated from January 2013 to January 2017 in Kunming Children's Hospital.Twenty patients were misdiagnosed in other hospital.After the routine examination of neck ultrasound and enhanced CT, internal fistula was found by self-retaining laryngoscope, traced by methylene blue, and excised by high ligation. Twenty patients were misdiagnosed.The misdiagnosis time ranged from 6 months to 3 years.Under self-retaining laryngoscope, piriform fossa fistula were found in all patients.Nineteen fistula were found in the left and 1 in the right.The fistula in patients was unilateral.Seven cases were misdiagnosed as suppurative lymphadensitis, undergone abscess incisional drainage many times.Three cases were misdiagnosed as thyroglossal duct cyst and performed excision of thyroglossal duct cyst.One case was treated by extended Sistruck operation again because the doctor considered that excision of middle segment of hyoid bone was not enough and the fistula was not ligated completely.One case was misdiagnosed as second branchial cleft fistula on the right side of the neck.Nine cases were misdiagnosed as hyroid-associated diseases including 2 cases suppurative thyroiditis, 2 cases subacute thyroiditis and 5 cases thyroid neoplasms.Among them, 2 cases underwent partial thyroidectomy.All the patients were treated with high ligation of fistula under general anesthesia.The operation was smooth, and no hoarseness, bucking and pharyngeal fistula occurred after the operation.Postoperative follow-up time ranged from 12 months to 4 years and the median follow-up was 18 months without recurrence.The diagnosis was confirmed pathologically. Pyriform sinus fistula in children was uncommon and easily misdiagnosed in clinic.The majority of physician including some otolaryngologists were lack of understanding of the disease.It should be regarded as one of the important differential diagnosis of neck mass in children.Children with recurrent left neck infection and/or abscess should be highly suspected.Self-retaining laryngoscopic examination can make a definite diagnosis and high ligation of the fistula through the external neck approach can achieve good therapeutic effect.
探讨梨状窝瘘的误诊情况,以更好地认识此类疾病。分析对象为2013年1月至2017年1月在昆明市儿童医院接受手术治疗的28例先天性梨状窝瘘患儿,年龄11个月至14岁,中位年龄5岁。20例曾在其他医院误诊。经颈部超声及增强CT常规检查后,通过支撑喉镜发现内瘘,以亚甲蓝追踪,行高位结扎切除。20例存在误诊情况,误诊时间为6个月至3年。在支撑喉镜下,所有患者均发现梨状窝瘘。左侧发现19例,右侧1例。患者的瘘为单侧。7例误诊为化脓性淋巴结炎,多次行脓肿切开引流。3例误诊为甲状舌管囊肿,行甲状舌管囊肿切除术。1例因医生认为舌骨中段切除不够、瘘管结扎不完全,再次行扩大Sistruck手术。1例误诊为右侧颈部第二鳃裂瘘。9例误诊为甲状腺相关疾病,其中化脓性甲状腺炎2例、亚急性甲状腺炎2例、甲状腺肿瘤5例。其中2例行甲状腺部分切除术。所有患者均在全身麻醉下行瘘管高位结扎术。手术顺利,术后未出现声音嘶哑、呛咳及咽瘘。术后随访时间为12个月至4年,中位随访时间为18个月,无复发。病理确诊。儿童梨状窝瘘临床少见,易误诊。包括部分耳鼻咽喉科医生在内的多数医生对此病认识不足。应将其视为儿童颈部肿块重要的鉴别诊断之一。对反复出现左侧颈部感染和/或脓肿的患儿应高度怀疑。支撑喉镜检查可明确诊断,经颈部外入路行瘘管高位结扎可取得良好治疗效果。