Wang Jin, Jiao Juyang, Zhao Guanglei, Shi Jingsheng, Xia Jun
Department of Orthopedics, Huashan Hospital, Fudan University, Shanghai, China.
Medicine (Baltimore). 2018 May;97(20):e10766. doi: 10.1097/MD.0000000000010766.
Focal myositis (FM) is a very rare myopathy of unknown etiology characterized by focal enlargement within one single skeletal muscle. In particular, it occurs only involving the Sartorius muscle has never been reported.
A 25-year-old man was admitted to the hospital with progressive restricted left hip joint extension, left thigh discomfort and gait disturbance for 6 years.
Combining clinical manifestations with results of radiological and pathological examinations, it was consistent with the diagnosis of FM INTERVENTIONS:: The patient received a surgery under general anesthesia to release the contracted Sartorius tendon.
The range of motion of the patient's left hip and ipsilateral knee has significantly improved as well as the discomfort of his left thigh relieved obviously after the surgery.
This case report is the first to report FM presenting as sartorius muscle contracture and the surgery is an alternative therapy for these patients.
局灶性肌炎(FM)是一种病因不明的极为罕见的肌病,其特征为单一骨骼肌内的局灶性肿大。特别是,仅累及缝匠肌的情况从未有过报道。
一名25岁男性因进行性左髋关节伸展受限、左大腿不适及步态障碍6年入院。
结合临床表现以及影像学和病理检查结果,符合FM的诊断。
患者在全身麻醉下接受手术,松解挛缩的缝匠肌腱。
术后患者左髋关节和同侧膝关节的活动范围明显改善,左大腿不适也明显缓解。
本病例报告首次报道了表现为缝匠肌挛缩的FM,手术是这些患者的一种替代治疗方法。