Inflammation division, The Walter and Eliza Hall Institute of Medical Research, Parkville, 3052, Australia.
Department of Medical Biology, University of Melbourne, Parkville, Victoria, 3010, Australia.
Curr Rheumatol Rep. 2018 May 30;20(7):40. doi: 10.1007/s11926-018-0750-4.
Autoinflammatory diseases are driven by abnormal innate immune activation. In the case of inflammasomopathies, these are all attributable to activation of an inflammasome complex, nucleated by an innate immune sensor such as NLRP3. This review will focus on recent advances that have helped to elucidate the role of three other sensors (NLRP1, NLRC4 and pyrin) which can also cause inflammasomopathies.
Mutations in pyrin (S242R or E244K) destroy an inhibitory 14-3-3 binding site and result in the newly characterised disease pyrin-associated autoinflammation with neutrophilic dermatosis (PAAND). Moreover, a separate autoinflammatory disease driven by mevalonate kinase deficiency leads to defective RhoGTPase prenylation and subsequent loss of pyrin S242R phosphorylation, suggesting a shared mechanism of disease. Other inflammasomes such as NLRP1 and NLRC4 have had novel mutations described recently, which inform about the specific domains required for activation and autoinhibition. This review covers recent advances in the study of inflammasomopathies, focussing on gene discoveries that elucidate new pathogenic mechanisms.
自身炎症性疾病是由异常先天免疫激活驱动的。在炎性小体病的情况下,这些都归因于炎性小体复合物的激活,该复合物由先天免疫传感器(如 NLRP3)核化。这篇综述将重点介绍最近的进展,这些进展有助于阐明其他三个也可引起炎性小体病的传感器(NLRP1、NLRC4 和 pyrin)的作用。
pyrin(S242R 或 E244K)的突变破坏了一个抑制性的 14-3-3 结合位点,导致新描述的疾病 pyrin 相关自身炎症伴中性粒细胞皮肤病(PAAND)。此外,由甲羟戊酸激酶缺乏引起的另一种自身炎症性疾病导致 RhoGTPase prenylation 缺陷和随后的 pyrin S242R 磷酸化缺失,表明存在共同的疾病机制。其他炎性小体,如 NLRP1 和 NLRC4,最近也有新的突变描述,这些描述提供了关于激活和自身抑制所需的特定结构域的信息。这篇综述涵盖了炎性小体病研究的最新进展,重点介绍了阐明新发病机制的基因发现。