Suzuki K, Miyamoto M, Miyamoto T, Matsubara T, Inoue Y, Iijima M, Mizuno S, Horie J, Hirata K, Shimizu T, Kanbayashi T
1 Department of Neurology, Dokkyo Medical University, Tochigi, Japan.
2 Department of Clinical Medicine for Nursing, Dokkyo Medical University School of Nursing, Tochigi, Japan.
Lupus. 2018 Oct;27(11):1847-1853. doi: 10.1177/0961203318778767. Epub 2018 May 31.
Objective Involvement of the hypothalamus is rare in patients with systemic lupus erythematosus (SLE). In this study, we measured cerebrospinal fluid (CSF) orexin-A levels in SLE patients with hypothalamic lesions to investigate whether the orexin system plays a role in SLE patients with hypothalamic lesions who present with excessive daytime sleepiness (EDS). Methods Orexin-A levels were measured in CSF from four patients with SLE who presented with hypothalamic lesions detected by MRI. Three patients underwent repeated CSF testing. All patients met the updated American College of Rheumatology revised criteria for SLE. Results Tests for serum anti-aquaporin-4 antibodies, CSF myelin basic protein and CSF oligoclonal bands were negative in all patients. All patients presented with EDS. Low to intermediate CSF orexin-A levels (92-180 pg/ml) were observed in three patients in the acute stage, two of whom (patients 1 and 2) underwent repeated testing and showed increased CSF orexin-A levels, reduced abnormal hypothalamic lesion intensities detected by MRI and EDS dissipation at follow-up. In contrast, CSF orexin-A levels were normal in one patient (patient 4) while in the acute stage and at follow-up, despite improvements in EDS and MRI findings. Patient 4 showed markedly increased CSF interleukin-6 levels (1130 pg/ml) and a slightly involved hypothalamus than the other patients. Conclusions Our findings suggest that the orexinergic system has a role in EDS in SLE patients with hypothalamic lesions. Furthermore, cytokine-mediated tissue damage might cause EDS without orexinergic involvement.
目的 系统性红斑狼疮(SLE)患者中下丘脑受累情况罕见。在本研究中,我们测量了患有下丘脑病变的SLE患者脑脊液(CSF)中食欲素-A水平,以调查食欲素系统在出现日间过度嗜睡(EDS)的患有下丘脑病变的SLE患者中是否起作用。方法 对4例经MRI检测出下丘脑病变的SLE患者的脑脊液进行食欲素-A水平测定。3例患者接受了重复的脑脊液检测。所有患者均符合美国风湿病学会修订的SLE最新标准。结果 所有患者血清抗水通道蛋白4抗体、脑脊液髓鞘碱性蛋白和脑脊液寡克隆带检测均为阴性。所有患者均出现EDS。3例急性期患者脑脊液食欲素-A水平为低至中等(92 - 180 pg/ml),其中2例(患者1和患者2)接受了重复检测,随访时脑脊液食欲素-A水平升高,MRI检测到的下丘脑病变异常强度降低且EDS消失。相比之下,1例患者(患者4)在急性期和随访时脑脊液食欲素-A水平正常,尽管其EDS和MRI表现有所改善。患者4脑脊液白细胞介素-6水平显著升高(1130 pg/ml),下丘脑受累程度略低于其他患者。结论 我们的研究结果表明,食欲素能系统在患有下丘脑病变的SLE患者的EDS中起作用。此外,细胞因子介导的组织损伤可能导致EDS而无需食欲素能系统参与。