Department of Hematology, National Cancer Center Hospital, 5-1-1 Tsukiji, Chuo-ku, Tokyo, 104-0045, Japan.
Department of Hematology, National Cancer Center Hospital East, Kashiwa, Japan.
Ann Hematol. 2019 Jan;98(1):131-142. doi: 10.1007/s00277-018-3418-2. Epub 2018 Jul 5.
Peripheral T cell lymphomas are an aggressive group of non-Hodgkin lymphomas with poor outcomes for most subtypes and no accepted standard of care for relapsed patients. This study evaluated the efficacy and safety of forodesine, a novel purine nucleoside phosphorylase inhibitor, in patients with relapsed peripheral T cell lymphomas. Patients with histologically confirmed disease, progression after ≥ 1 prior treatment, and an objective response to last treatment received oral forodesine 300 mg twice-daily. The primary endpoint was objective response rate (ORR). Secondary endpoints included duration of response, progression-free survival (PFS), overall survival (OS), and safety. Forty-eight patients (median age, 69.5 years; median of 2 prior treatments) received forodesine. In phase 1 (n = 3 evaluable), no dose-limiting toxicity was observed during the first 28 days of forodesine treatment. In phase 2 (n = 41 evaluable), the ORR for the primary and final analyses was 22% (90% CI 12-35%) and 25% (90% CI 14-38%), respectively, including four complete responses (10%). Median PFS and OS were 1.9 and 15.6 months, respectively. The most common grade 3/4 adverse events were lymphopenia (96%), leukopenia (42%), and neutropenia (35%). Dose reduction and discontinuation due to adverse events were uncommon. Secondary B cell lymphoma developed in five patients, of whom four were positive for Epstein-Barr virus. In conclusion, forodesine has single-agent activity within the range of approved therapies in relapsed peripheral T cell lymphomas, with a manageable safety profile, and may represent a viable treatment option for this difficult-to-treat population.
外周 T 细胞淋巴瘤是一组侵袭性非霍奇金淋巴瘤,大多数亚型的预后较差,且复发患者尚无公认的标准治疗方法。本研究评估了新型嘌呤核苷磷酸化酶抑制剂氟达拉滨在复发外周 T 细胞淋巴瘤患者中的疗效和安全性。组织学确诊疾病、≥1 次既往治疗后进展且上次治疗有客观缓解的患者接受氟达拉滨 300mg,每日 2 次口服。主要终点为客观缓解率(ORR)。次要终点包括缓解持续时间、无进展生存期(PFS)、总生存期(OS)和安全性。48 例(中位年龄 69.5 岁;中位既往治疗 2 次)患者接受了氟达拉滨治疗。在 1 期(n=3 例可评估)中,氟达拉滨治疗的前 28 天未观察到剂量限制毒性。在 2 期(n=41 例可评估)中,主要和最终分析的 ORR 分别为 22%(90%CI 12-35%)和 25%(90%CI 14-38%),包括 4 例完全缓解(10%)。中位 PFS 和 OS 分别为 1.9 和 15.6 个月。最常见的 3/4 级不良事件为淋巴细胞减少(96%)、白细胞减少(42%)和中性粒细胞减少(35%)。因不良事件而减少剂量和停药的情况并不常见。5 例患者发生继发性 B 细胞淋巴瘤,其中 4 例 EBV 阳性。结论:氟达拉滨在外周 T 细胞淋巴瘤复发患者中具有在批准的治疗范围内的单药活性,具有可管理的安全性,可能是这一治疗困难人群的可行治疗选择。