Kim Hyeon Su, Kim Na Young, Kim Yong Wook
Department and Research Institute of Rehabilitation Medicine, College of Medicine, Yonsei University, Seoul, Republic of Korea.
Clin Neuropharmacol. 2018 Jul/Aug;41(4):138-141. doi: 10.1097/WNF.0000000000000289.
Paroxysmal sympathetic hyperactivity (PSH) is characterized by increased activity of the sympathetic nervous system. Although several treatments have been proposed for PSH, their efficacies are uncertain. We report a case of a patient with intractable PSH after pontine hemorrhage who was treated with intrathecal baclofen (ITB). A 61-year-old man was diagnosed with pontine hemorrhage expanding to the bilateral midbrain. Beginning 2 weeks after onset, he developed paroxysmal hyperthermia, tachycardia, tachypnea, hypertension, and generalized dystonic movements. Several medications were administered to the patient, including fentanyl patch, dantrolene, gabapentin, and β blockers. Nevertheless, PSH episodes continued to occur more than twice per day. Seven months after onset, we performed a trial of ITB injection, which led to reduced severity and frequency of PSH. Therefore, the ITB therapy was implanted. Continuous ITB was initiated at a rate of 100 μg/d, which was gradually increased up to 200 μg/d. Oral medications were tapered off. No PSH episode occurred for 4 weeks. Our findings suggest that ITB therapy may be used to manage intractable PSH. Intrathecal baclofen may inhibit postsynaptic activity and suppress sympathetic activity via the stimulation of γ-aminobutyric acid B receptors the brain.
阵发性交感神经过度兴奋(PSH)的特征是交感神经系统活动增强。尽管已提出多种治疗PSH的方法,但其疗效尚不确定。我们报告一例桥脑出血后难治性PSH患者接受鞘内注射巴氯芬(ITB)治疗的病例。一名61岁男性被诊断为桥脑出血并扩展至双侧中脑。发病2周后,他出现阵发性高热、心动过速、呼吸急促、高血压和全身性肌张力障碍运动。患者接受了多种药物治疗,包括芬太尼透皮贴剂、丹曲林、加巴喷丁和β受体阻滞剂。然而,PSH发作仍每天发生两次以上。发病7个月后,我们进行了ITB注射试验,结果PSH的严重程度和发作频率降低。因此,植入了ITB治疗装置。以100μg/d的速率开始持续ITB治疗,并逐渐增加至200μg/d。口服药物逐渐减量。4周内未发生PSH发作。我们的研究结果表明,ITB治疗可用于治疗难治性PSH。鞘内注射巴氯芬可能通过刺激大脑中的γ-氨基丁酸B受体来抑制突触后活动并抑制交感神经活动。