Neurogenetics Unit, 1st Department of Neurology, Eginition Hospital, Medical School, National and Kapodistrian University of Athens, 72-74 Vasilissis Sofias, 11528, Athens, Greece.
J Neurol. 2019 Mar;266(3):565-573. doi: 10.1007/s00415-018-8968-7. Epub 2018 Jul 13.
Spinal and bulbar muscular atrophy (SBMA), also known as Kennedy's disease, is a rare, X-linked hereditary lower motor neuron disease, characterized by progressive muscular weakness. An expanded trinucleotide repeat (CAG > 37) in the androgen receptor gene (AR), encoding glutamine, is the mutation responsible for Kennedy's disease. Toxicity of this mutant protein affects both motor neurons and muscles. In this review, we provide a comprehensive, clinically oriented overview of the current literature regarding Kennedy's disease, highlighting gaps in our knowledge that remain to be addressed in further research. Kennedy's disease mimics are also discussed, as are ongoing and recently completed therapeutic endeavours.
脊髓延髓肌萎缩症(SBMA),又称肯尼迪病,是一种罕见的 X 连锁遗传性下运动神经元疾病,其特征是进行性肌肉无力。雄激素受体基因(AR)中三核苷酸重复序列(CAG > 37)的扩展,编码谷氨酰胺,是导致肯尼迪病的突变。这种突变蛋白的毒性影响运动神经元和肌肉。在这篇综述中,我们提供了关于肯尼迪病的当前文献的全面、以临床为导向的概述,强调了在进一步研究中仍需解决的知识空白。我们还讨论了肯尼迪病的模拟疾病,以及正在进行和最近完成的治疗努力。