Suppr超能文献

韩国一名早发性阿尔茨海默病伴帕金森病患者中新型 PSEN1 p.Gly417Ala 突变。

Novel PSEN1 p.Gly417Ala mutation in a Korean patient with early-onset Alzheimer's disease with parkinsonism.

机构信息

Department of BioNano Technology, Gachon Medical Research Institute, Gachon University, Sungnam, South Korea.

Department of Neurology, Roa Neurology Clinic, Seongnam-si, Gyeonggi-do, Republic of Korea.

出版信息

Neurobiol Aging. 2018 Dec;72:188.e13-188.e17. doi: 10.1016/j.neurobiolaging.2018.08.003. Epub 2018 Aug 9.

Abstract

Mutations in presenilin 1 (PSEN1) are the most common cause of autosomal dominant Alzheimer's disease. Here, we report a 37-year-old male Korean patient carrying a PSEN1 p.Gly417Ala mutation with exceptionally early and severe presentations, including a wide range of atypical symptoms of rapid cognitive decline with a stooped posture, rigidity, and bradykinesia. Targeted next-generation sequencing of proband revealed a novel nucleotide substitution (c.1250G>C) in exon 12 of PSEN1 gene, altering glycine to alanine at 417 position. Three-dimensional protein structure prediction revealed that the variant may cause perturbations in the 8th transmembrane region, perturbing its functions from the increased hydrophobicity and size of alanine with decreased flexibility. Since several glycine>alanine substitutions in other PSEN1 transmembrane helices revealed aggressive Alzheimer's disease phenotypes, PSEN1 Gly417Ala may share a common pathogenic mechanism.

摘要

早老素 1 基因突变(PSEN1)是最常见的常染色体显性遗传性阿尔茨海默病的病因。在这里,我们报告了一例韩国 37 岁男性患者,携带早老素 1 p.Gly417Ala 突变,具有异常早发和严重的表现,包括广泛的非典型快速认知衰退症状,伴有弯腰姿势、僵硬和运动迟缓。对先证者进行靶向下一代测序发现 PSEN1 基因第 12 外显子的一个新核苷酸取代(c.1250G>C),导致第 417 位的甘氨酸被丙氨酸取代。三维蛋白质结构预测表明,该变体可能导致第 8 个跨膜区域的扰动,从而改变其功能,增加丙氨酸的疏水性和大小,降低其灵活性。由于其他早老素 1 跨膜螺旋中的几个甘氨酸>丙氨酸取代揭示了侵袭性阿尔茨海默病表型,PSEN1 Gly417Ala 可能具有共同的发病机制。

文献AI研究员

20分钟写一篇综述,助力文献阅读效率提升50倍。

立即体验

用中文搜PubMed

大模型驱动的PubMed中文搜索引擎

马上搜索

文档翻译

学术文献翻译模型,支持多种主流文档格式。

立即体验