Pierson M, Leheup B
Hôpital d'Enfants, CHU Nancy-Brabois, Vandoeuvre-les-Nancy.
J Genet Hum. 1988 Jun;36(3):181-99.
Among the group of hereditary histodysplasia, Bourneville's tuberous sclerosis demonstrate original and important place. Its clinical and histopathological polymorphism make more difficult the diagnosis because many symptoms are non specific and/or appeared at different age of life. The variability of the expression and of the penetrance are a very serious unpeachement for the genetic counselling. A recent reevaluation of several series of case reports seems to demonstrate that the frequency of new mutations has been probably surestimated. The gene location in 9q3-4 is quite certain and will induce soon the possibility of a more efficient prenatal diagnosis. The gene action mechanism at the embryonic development is probably correlated with the "oncogene character" of the specific mutation.
在遗传性组织发育异常组中,结节性硬化症(Bourneville病)占有独特且重要的地位。其临床和组织病理学的多态性使诊断变得更加困难,因为许多症状是非特异性的和/或出现在生命的不同阶段。表达和外显率的变异性给遗传咨询带来了非常严重的障碍。最近对几组病例报告的重新评估似乎表明,新突变的频率可能被高估了。位于9q3 - 4的基因定位相当确定,这将很快带来更有效的产前诊断的可能性。该基因在胚胎发育中的作用机制可能与特定突变的“癌基因特征”相关。