Khanna Kashish, Khanna Vikram, Bhatnagar Veereshwar
Department of Pediatric Surgery, All India Institute of Medical Sciences, New Delhi, Delhi, India.
Department of Pediatric Surgery, Lady Hardinge Medical College, New Delhi, Delhi, India.
BMJ Case Rep. 2018 Dec 13;11(1):e225076. doi: 10.1136/bcr-2018-225076.
Peutz-Jeghers syndrome (PJS) is an autosomal dominant cancer-predisposing condition characterised by intestinal hamartomatous polyps and distinct melanin depositions in skin and mucosa. Small intestinal cancer in patients with PJS usually presents by the third decade. A 7-year-old-PJS boy presented with recurrent episodes of colicky abdominal pain and melena requiring repeated blood transfusions. Abdominal CT scan revealed multiple jejunal polyps with jejunoileal intussusception. On exploration, the intussuscepted bowel was resected along with its mesentery and anastomosed. Simultaneously, multiple enterotomies with resection of palpable polyps were performed. The resected bowel showed well-differentiated stage 2A adenocarcinoma with clear resected margins. Postoperatively, the complaints were relieved. On follow-up, he was asymptomatic and is now on yearly cancer surveillance. This is probably the youngest reported case of small bowel cancer in PJS.
佩-吉综合征(PJS)是一种常染色体显性遗传性癌症易感疾病,其特征为肠道错构瘤性息肉以及皮肤和黏膜中独特的黑色素沉着。PJS患者的小肠癌通常在第三个十年出现。一名7岁的PJS男孩出现反复的绞痛性腹痛和黑便,需要反复输血。腹部CT扫描显示多个空肠息肉伴空肠回肠套叠。手术探查时,将套叠的肠段及其系膜一并切除并进行吻合。同时,进行了多处肠切开术并切除可触及的息肉。切除的肠段显示为高分化2A期腺癌,切缘清晰。术后,症状得到缓解。随访时,他无症状,目前每年接受癌症监测。这可能是报道的PJS患者中最年轻的小肠癌病例。