UCL Great Ormond Street Hospital Institute of Child Health, 30 Guilford Street, London, WC1N 1EH, UK.
Paediatr Drugs. 2019 Feb;21(1):1-13. doi: 10.1007/s40272-018-0323-z.
Although differences exist in treatment and risk-stratification strategies for children with Wilms tumor (WT) between the European [International Society of Paediatric Oncology (SIOP)] and American [Children's Oncology Group (COG)] study groups, outcomes are very similar, with an overall survival of > 85%. Future strategies aim to de-intensify treatment and reduce toxicity for children with a low risk of relapse and intensify treatment for children with high-risk disease. For metastatic WT, response of lung nodules to chemotherapy is used as a marker to modify treatment intensity. For recurrent WT, a unified approach based on the use of agents that were not used for primary therapy is being introduced. Irinotecan is being explored as a new strategy in both metastatic and relapsed WT. Introduction of biology-driven approaches to risk stratification and new drug treatments has been slower in WT than in some other childhood cancers. While several new biological pathways have been identified recently in WT, their individual rarity has hampered their translation into clinical utility. Identification of robust prognostic factors requires extensive international collaborative studies because of the low proportion who relapse or die. Molecular profiling studies are in progress that should ultimately improve both risk classification and signposting to more targeted therapies for the small group for whom current therapies fail. Accrual of patients with WT to early-phase trials has been low, and the efficacy of these new agents has so far been very disappointing. Better in vitro model systems to test mechanistic dependence are needed so available new agents can be more rationally prioritized for recruitment of children with WT to early-phase trials.
尽管欧洲 [国际小儿肿瘤学会 (SIOP)] 和美国 [儿童肿瘤学组 (COG)] 研究组在儿童肾母细胞瘤 (WT) 的治疗和风险分层策略上存在差异,但结果非常相似,总体生存率 > 85%。未来的策略旨在为复发风险低的儿童减轻治疗强度并降低毒性,并为高危疾病的儿童强化治疗。对于转移性 WT,肺部结节对化疗的反应被用作调整治疗强度的标志物。对于复发性 WT,正在引入一种基于使用原发性治疗未使用的药物的统一方法。伊立替康正在转移性和复发性 WT 中作为一种新策略进行探索。与其他一些儿童癌症相比,WT 中生物学驱动的风险分层和新药治疗的引入速度较慢。虽然最近在 WT 中发现了几个新的生物学途径,但它们各自的罕见性阻碍了它们转化为临床应用。需要进行广泛的国际合作研究来确定可靠的预后因素,因为复发或死亡的比例较低。正在进行分子谱研究,最终应改善风险分类,并为目前治疗失败的少数患者提供更有针对性的治疗。WT 患者入组早期试验的比例一直很低,这些新药物的疗效迄今为止非常令人失望。需要更好的体外模型系统来测试机制依赖性,以便可以更合理地优先招募 WT 患儿参加早期试验。