Takahashi Saori, Idaira Yayoi, Sato Toru, Asada Yoshinobu, Nakagawa Yoichi
J Clin Pediatr Dent. 2019;43(2):121-125. doi: 10.17796/1053-4625-43.2.9. Epub 2019 Feb 7.
Unicystic ameloblastoma (UAM) is a variant of intraosseous ameloblastoma that occurs as a single cystic cavity. This report describes a case of UAM of the mandible in a seven-year-old girl. The lesion radiographically mimicked a dentigerous cyst. Under the primary diagnosis of a dentigerous cyst, marsupialization was performed to erupt the first molar involved in the cystic lesion and to obtain a definitive diagnosis. The biopsy specimen revealed ameloblastoma. During careful observation, orthodontic treatment, which was performed to upright and promote the eruption of the first molar involved in the tumor, maintained the space needed for enucleation of the tumor. Finally, the second primary molar was extracted, and the lesion was enucleated at 3 years and 4 months after marsupialization. The results of the histological examination revealed UAM. Conclusively, the treatment course not only avoids a resection of the mandible but also induces eruption of the teeth involved in the tumor. Thus, the combination of conservative surgery and orthodontic treatment was effective in the management of UAM that mimics a dentigerous cyst.
单囊性成釉细胞瘤（UAM）是骨内成釉细胞瘤的一种变体，表现为单个囊腔。本报告描述了一名7岁女孩下颌骨单囊性成釉细胞瘤的病例。该病变在影像学上类似含牙囊肿。在初步诊断为含牙囊肿的情况下，进行了袋形术，以使囊肿性病变累及的第一磨牙萌出，并获得明确诊断。活检标本显示为成釉细胞瘤。在仔细观察期间，为使肿瘤累及的第一磨牙直立并促进其萌出而进行的正畸治疗，维持了肿瘤摘除所需的间隙。最后，拔除了第二乳磨牙，并在袋形术后3年4个月摘除了病变。组织学检查结果显示为单囊性成釉细胞瘤。总之，该治疗过程不仅避免了下颌骨切除，还促使肿瘤累及的牙齿萌出。因此，保守手术与正畸治疗相结合在治疗类似含牙囊肿的单囊性成釉细胞瘤方面是有效的。
