Nettleton Jeremy, Crawford-Smith Hugh, Adimonye Anthony, McMeekin Faith
Department of Urology, Gloucestershire Hospitals NHS Foundation Trust, Cheltenham, UK.
BMJ Case Rep. 2019 Feb 21;12(2):e226530. doi: 10.1136/bcr-2018-226530.
Juvenile gangrenous vasculitis of the scrotum is a rare entity, of which to our knowledge we describe the first documented case in the UK. It follows a typical disease course, demonstrated by an 18-year-old male who presented with three necrotic scrotal lesions; proceeded by 3 days of fever, pharyngitis and lethargy. Previous cases have been managed successfully with systemic steroids. On this occasion, surgical debridement was made of the necrotic areas under antibiotic cover and complete resolution was achieved with excellent wound healing and no evidence of recurrence. This case report discusses the importance of disease recognition and the merits of surgical management. We also add to the debate as to whether this disease is a variation of pyoderma gangrenosum or a distinct entity itself within the pantheon of scrotal gangrene.
青少年阴囊坏疽性血管炎是一种罕见疾病,据我们所知,我们描述了英国首例有记录的病例。它呈现出典型的病程,一名18岁男性患者表现为阴囊有三处坏死性病变;在此之前有3天的发热、咽炎和嗜睡症状。既往病例通过全身使用类固醇已成功治愈。此次,在抗生素覆盖下对坏死区域进行了手术清创,伤口愈合良好,完全康复,且无复发迹象。本病例报告讨论了疾病识别的重要性以及手术治疗的优点。我们还加入了关于该疾病是坏疽性脓皮病的一种变异还是阴囊坏疽范畴内一种独特疾病的争论。