Weisinger J R, Mogollón A, Lander R, Bellorin-Font E, Riera R, Abadí I, Paz-Martínez V
Arch Intern Med. 1986 Mar;146(3):473-7.
Extensive bilateral cerebral cortical calcifications were demonstrated in a young patient with a history of convulsions since the age of 4 years. Initial metabolic workup showed normal serum calcium levels, hyperphosphatemia, normal renal function, low urinary calcium excretion, and normal serum immunoreactive parathyroid hormone levels. The intravenous infusion of edetate disodium (disodium EDTA) showed a normal phosphaturic and cyclic adenosine monophosphate response, ruling out the diagnosis of pseudohypoparathyroidism. The infusion of acetazolamide produced a blunted phosphaturia with almost no change in the renal phosphorus threshold, suggesting a tubular defect that allows enhanced proximal tubular reabsorption of phosphorus. Although the exact mechanisms responsible for the localized calcifications remain obscure, we suggest that an enhanced proximal tubular reabsorption of phosphorus could be involved in the pathophysiologic basis of this abnormality.
一名自幼(4岁起)有惊厥病史的年轻患者经检查发现双侧大脑皮质广泛钙化。初始代谢检查显示血清钙水平正常、高磷血症、肾功能正常、尿钙排泄低以及血清免疫反应性甲状旁腺激素水平正常。静脉输注依地酸二钠(乙二胺四乙酸二钠)显示磷尿和环磷酸腺苷反应正常,排除了假性甲状旁腺功能减退的诊断。输注乙酰唑胺导致磷尿减弱,肾磷阈值几乎无变化,提示存在肾小管缺陷,使得近端肾小管对磷的重吸收增强。尽管导致局部钙化的确切机制仍不清楚,但我们认为近端肾小管对磷的重吸收增强可能参与了这种异常的病理生理基础。