Research and Development, Vifor Pharma Group, Glattbrugg, Switzerland.
Early Development Services, PRA Health Sciences, Groningen, Netherlands.
Am J Hematol. 2020 Jan;95(1):68-77. doi: 10.1002/ajh.25670. Epub 2019 Nov 19.
Restriction of iron availability by ferroportin inhibition is a novel approach to treating non-transfusion-dependent thalassemia (β-thalassemia intermedia). This first-in-human, Phase I study (https://www.clinicaltrialsregister.eu; EudraCT no. 2017-003395-31) assessed the safety, tolerability, pharmacokinetics and pharmacodynamics of single- and multiple-ascending doses (SAD and MAD) of the oral ferroportin inhibitor, VIT-2763, in healthy volunteers. Participants received VIT-2763 5/15/60/120/240 mg or placebo in the SAD phase and VIT-2763 60/120 mg once daily, VIT-2763 60/120 mg twice daily, or placebo for 7 days in the MAD phase. Seventy-two participants completed treatment. VIT-2763 was well tolerated and demonstrated a similar safety profile to the placebo. There were no serious or severe adverse events, or discontinuations due to adverse events. VIT-2763 absorption was relatively fast, with detectable levels 15 to 30 minutes post-dose. Following multiple dosing there was no apparent change in absorption and accumulation was minimal. Mean elimination half-life was 1.9 to 5.3 hours following single dosing, and 2.1 to 3.8 hours on Day 1 and 2.6 to 5.3 hours on Day 7, following repeated dosing. There was a temporary decrease in mean serum iron levels with VIT-2763 single doses ≥60 mg and all multiple doses; mean calculated transferrin saturation (only assessed following multiple dosing) also temporarily decreased. A shift in mean serum hepcidin peaks followed administration of all iron-lowering doses of VIT-2763. This effect was less pronounced after 7 days of multiple dosing (aside from with 120 mg once daily). These results support the initiation of clinical studies in patients with non-transfusion-dependent thalassemia and documented iron overload due to ineffective erythropoiesis.
通过抑制铁输出蛋白来限制铁的可用性是治疗非输血依赖型地中海贫血(中间型β地中海贫血)的一种新方法。这项首次人体、I 期研究(https://www.clinicaltrialsregister.eu;EudraCT 编号 2017-003395-31)评估了健康志愿者单次和多次递增剂量(SAD 和 MAD)口服铁输出蛋白抑制剂 VIT-2763 的安全性、耐受性、药代动力学和药效学。参与者在 SAD 阶段接受 VIT-2763 5/15/60/120/240mg 或安慰剂,在 MAD 阶段接受 VIT-2763 60/120mg 每日一次、VIT-2763 60/120mg 每日两次或安慰剂连续 7 天。72 名参与者完成了治疗。VIT-2763 耐受性良好,与安慰剂具有相似的安全性。没有严重或严重不良事件,也没有因不良事件而停药。VIT-2763 吸收较快,给药后 15 至 30 分钟即可检测到。多次给药后,吸收没有明显变化,蓄积最小。单次给药后平均消除半衰期为 1.9 至 5.3 小时,第 1 天和第 2 天重复给药后为 2.1 至 3.8 小时,第 7 天重复给药后为 2.6 至 5.3 小时。VIT-2763 单剂量≥60mg 和所有多剂量都会导致平均血清铁水平暂时下降;仅在多次给药后评估的平均计算转铁蛋白饱和度也暂时下降。所有铁降低剂量的 VIT-2763 给药后,平均血清肝素峰值发生转移。重复给药 7 天后,这种影响(除了 120mg 每日一次)不那么明显。这些结果支持对非输血依赖型地中海贫血和因无效红细胞生成导致铁过载的患者开始进行临床研究。