Department of Cardiology, Affiliated Drum Tower Hospital, Nanjing University School of Medicine, Nanjing, China.
Sci Rep. 2020 Feb 10;10(1):2226. doi: 10.1038/s41598-020-58984-7.
Dilated cardiomyopathy (DCM) is one of the leading causes of heart failure. A large proportion of genetic cause remains unexplained, especially in idiopathic DCM. We performed target next-generation sequencing of 102 genes which were known causes or candidate genes for cardiomyopathies and channelpathies in 118 prospectively recruited Han Chinese patients with idiopathic DCM. 41 of the 118 patients carried 40 pathogenic or likely pathogenic variants, providing a molecular diagnosis in 34.7% of patients. 32 of these variants were novel. TTN truncating variants were predominant, with a frequency of 31.0%, followed by variants of LMNA (14.3%), RBM20 (4.8%), and NEXN (4.8%). These 4 genes accounted for over half variants identified. No significant difference in clinical characteristics or rates of reaching the composite end point (cardiac transplantation and death from cardiac causes) between pathogenic or likely pathogenic variant carriers and noncarriers (hazard ratio 1.11, 95% CI: 0.41 to 3.00), or between patients with TTN truncating variants or without (hazard ratio 0.49, 95% CI: 0.36 to 6.10). In our prospective study, we first determined the overall genetic profiles and genotype-phenotype correlations in Han Chinese idiopathic DCM patients, which could provide insight for genetic diagnosis of DCM in this population.
扩张型心肌病(DCM)是心力衰竭的主要原因之一。很大一部分遗传原因仍未得到解释,尤其是特发性 DCM。我们对 118 名前瞻性招募的汉族特发性 DCM 患者的 102 个已知心肌病和通道病的致病基因或候选基因进行了靶向下一代测序。在这 118 名患者中,有 41 名携带 40 种致病性或可能致病性变异,其中 34.7%的患者获得了分子诊断。其中 32 种变异是新发现的。TTN 截断变异是主要类型,占 31.0%,其次是 LMNA(14.3%)、RBM20(4.8%)和 NEXN(4.8%)变异。这 4 个基因占所鉴定变异的一半以上。致病性或可能致病性变异携带者和非携带者之间的临床特征或复合终点(心脏移植和心脏原因死亡)发生率没有显著差异(危险比 1.11,95%可信区间:0.41 至 3.00),或 TTN 截断变异携带者和非携带者之间(危险比 0.49,95%可信区间:0.36 至 6.10)。在我们的前瞻性研究中,我们首先确定了汉族特发性 DCM 患者的总体遗传特征和基因型-表型相关性,这可为该人群的 DCM 遗传诊断提供参考。