ISR-Lisboa/LARSyS and Department of Bioengineering, Instituto Superior Técnico, Universidade de Lisboa, Lisbon, Portugal.
Neurological Imaging Department, Hospital de Santa Maria - CHULN, Lisbon, Portugal.
J Huntingtons Dis. 2020;9(2):143-148. doi: 10.3233/JHD-190388.
Huntington's disease (HD) is an autosomal-dominant neurodegenerative disorder inducing motor, psychiatric changes and cognitive decline, characterized pathologically by striatal atrophy. Pathological changes in the extra-striatal structures, such as the substantia nigra (SN), and abnormalities in pre-synaptic striatal dopamine neurotransmission are also known to occur. Neuromelanin (NM)-sensitive magnetic resonance imaging (NM-MRI) is an innovative technique that was recently developed allowing the in vivo study of pathological changes in the dopaminergic neurons of the SN.
To investigate the SN MR signal in HD patients.
We performed a cross-sectional study using a specific T1-weighted MR sequence to visualize NM. The areas and signal intensity contrast ratios of the T1 hyperintense SN regions were obtained using a semi-automatic segmentation method.
A total of 8 HD patients and 12 healthy subjects were evaluated. The SN area was markedly reduced in the HD group compared with the control group (p = 0.02), even after normalization of the SN area with the midbrain area and age correction (p = 0.01). There was a significant reduction in the intensity contrast ratio of the hyperintense SN areas to crus cerebri in HD patients comparing with controls (p = 0.04) after correction for age.
NM-sensitive MR techniques were used for the first time to study the SN in HD patients, showing loss of NM in this region, supporting the implication of dopaminergic neuronal changes in disease pathology. Future research needs to be conducted to evaluate the potential of SN area and intensity contrast as biomarkers for HD.
亨廷顿病(HD)是一种常染色体显性遗传的神经退行性疾病,可引起运动、精神变化和认知能力下降,其病理学特征为纹状体萎缩。已知在纹状体以外的结构(如黑质)中存在病理性变化,以及前纹状体多巴胺神经递质传递的异常。神经黑色素(NM)敏感磁共振成像(NM-MRI)是一种创新性技术,最近已被开发出来,可用于活体研究黑质多巴胺能神经元的病理性变化。
研究亨廷顿病患者的黑质磁共振信号。
我们使用一种特定的 T1 加权磁共振序列进行了一项横断面研究,以可视化 NM。使用半自动分割方法获得 T1 高信号黑质区域的面积和信号强度对比比值。
共评估了 8 名 HD 患者和 12 名健康受试者。与对照组相比,HD 组的黑质面积明显减小(p=0.02),即使在对黑质面积与中脑面积和年龄校正后也是如此(p=0.01)。校正年龄后,HD 患者的高信号黑质区域与大脑脚之间的强度对比比值显著降低(p=0.04)。
首次使用 NM 敏感磁共振技术研究 HD 患者的黑质,显示该区域 NM 丢失,支持多巴胺能神经元变化在疾病病理学中的作用。需要进一步研究以评估黑质面积和强度对比作为 HD 生物标志物的潜力。