Department of Life Science, National Taiwan Normal University, Taipei, Taiwan.
Department of Nursing, Mackay Junior College of Medicine, Nursing and Management, Taipei, Taiwan.
J Mol Neurosci. 2020 Jul;70(7):1140-1152. doi: 10.1007/s12031-020-01521-y. Epub 2020 Mar 13.
Many protein aggregation diseases (PAD) affect the nervous system. Deposits of aggregated disease-specific proteins are found within or around the neuronal cells of neurodegenerative diseases. Although the main protein component is disease-specific, oligomeric aggregates are presumed to be the key agents causing the neurotoxicity. Evidence has shown that protein aggregates cause a chronic inflammatory reaction in the brain, resulting in neurodegeneration. Therefore, strategies targeting anti-inflammation could be beneficial to the therapeutics of PAD. PHA-767491 was originally identified as an inhibitor of CDC7/CDK9 and was found to reduce TDP-43 phosphorylation and prevent neurodegeneration in TDP-43 transgenic animals. We recently identified PHA-767491 as a GSK-3β inhibitor. In this study, we established mouse hippocampal primary culture with tau-hyperphosphorylation through the activation of GSK-3β using Wortmannin and GF109203X. We found that PHA-767491 significantly improved the neurite outgrowth of hippocampal primary neurons against the neurotoxicity induced by GSK-3β. We further showed that PHA-767491 had neuroprotective ability in hippocampal primary culture under oligomeric Aβ treatment. In addition, PHA-767491 attenuated the neuroinflammation in mouse cerebellar slice culture with human TBP-109Q agitation. Further study of SCA17 transgenic mice carrying human TBP-109Q showed that PHA-767491 ameliorated the gait ataxia and the inflammatory response both centrally and peripherally. Our findings suggest that PHA-767491 has a broad spectrum of activity in the treatment of different PAD and that this activity could be based on the anti-inflammation mechanism.
许多蛋白质聚集疾病(PAD)会影响神经系统。神经退行性疾病的神经元细胞内或周围会发现聚集疾病特异性蛋白的沉积物。虽然主要的蛋白质成分是特异性的,但寡聚体聚集物被认为是引起神经毒性的关键因素。有证据表明,蛋白质聚集物会在大脑中引起慢性炎症反应,导致神经退行性变。因此,靶向抗炎的策略可能对 PAD 的治疗有益。PHA-767491 最初被鉴定为 CDC7/CDK9 的抑制剂,并且在 TDP-43 转基因动物中发现可减少 TDP-43 的磷酸化并预防神经退行性变。我们最近发现 PHA-767491 是一种 GSK-3β抑制剂。在这项研究中,我们使用 Wortmannin 和 GF109203X 通过激活 GSK-3β 在小鼠海马原代培养物中建立 tau 过度磷酸化。我们发现 PHA-767491 可显著改善 GSK-3β 诱导的神经毒性对海马原代神经元轴突生长的影响。我们进一步表明,PHA-767491 在寡聚体 Aβ 处理下的海马原代培养物中具有神经保护能力。此外,PHA-767491 可减轻人 TBP-109Q 搅拌的小脑切片培养中的神经炎症。进一步研究携带人 TBP-109Q 的 SCA17 转基因小鼠表明,PHA-767491 可改善中枢和外周的步态共济失调和炎症反应。我们的研究结果表明,PHA-767491 在治疗不同 PAD 方面具有广泛的活性,这种活性可能基于抗炎机制。