Dirar Qais S, Musalem Hebah M, Al-Hazzaa Selwa A F, Al Zoba Abdulaziz A, Almalki Amal A
College of Medicine, Alfaisal University, Riyadh, Saudi Arabia.
Department of Ophthalmology, King Faisal Specialist Hospital and Research Center, Riyadh, Saudi Arabia.
Am J Case Rep. 2020 Apr 6;21:e921301. doi: 10.12659/AJCR.921301.
BACKGROUND Xeroderma pigmentosum (XP) is an autosomal recessive disease caused by mutations in DNA repair genes. Clinical manifestations include extreme sensitivity to ultraviolet (UV) rays, freckle-like pigmentation, ocular abnormalities, and an increased risk of developing neoplasms in sun-exposed areas of the skin, mucous membranes, and eyes. This paper describes the clinical outcome of pegylated interferon alpha 2b (PEG-IFN-alpha-2b) subconjunctival injections and topical mitomycin C (MMC) in the treatment of ocular surface squamous neoplasia (OSSN) in patients with XP. CASE REPORT A series of 3 patients with histopathologically-proven biopsy specimens of XP-associated neoplasia of the eyelids and ocular surface underwent subconjunctival injections of PEG-IFN-alpha-2 band topical cycles of MMC. There was a noticeable decrease in the size and severity of ocular surface squamous neoplasia, with minimal adverse effects of flu-like symptoms with mild fever and generalized malaise. Transient mental depression was reported in 2 of our patients, and only 1 patient developed autoimmune diabetes mellitus, which required insulin therapy after the discontinuation of the PEG-IFN-alpha-2b. CONCLUSIONS The literature on the specifics of ocular care using PEG-IFN-alpha-2b for XP-associated OSSN is sparse. However, according to our clinical experience, the combination of PEG-IFN-alpha-2b subconjunctival injection and the topical cycles of MMC is a promising long-term medical therapy to minimize the development and recurrence of OSSN in XP patients.
背景 着色性干皮病(XP)是一种由DNA修复基因发生突变引起的常染色体隐性疾病。临床表现包括对紫外线(UV)极度敏感、雀斑样色素沉着、眼部异常,以及在皮肤、黏膜和眼睛的阳光暴露部位发生肿瘤的风险增加。本文描述了聚乙二醇化干扰素α-2b(PEG-IFN-α-2b)结膜下注射和局部使用丝裂霉素C(MMC)治疗XP患者眼表鳞状上皮肿瘤(OSSN)的临床结果。病例报告 3例经组织病理学证实为眼睑和眼表XP相关肿瘤活检标本的患者接受了PEG-IFN-α-2b结膜下注射和MMC局部治疗周期。眼表鳞状上皮肿瘤的大小和严重程度明显降低,出现的不良反应为类似流感的症状,伴有低热和全身不适。我们的2例患者报告有短暂的精神抑郁,只有1例患者发生自身免疫性糖尿病,在停用PEG-IFN-α-2b后需要胰岛素治疗。结论 关于使用PEG-IFN-α-2b治疗XP相关OSSN的眼部护理具体情况的文献很少。然而,根据我们的临床经验,PEG-IFN-α-2b结膜下注射与MMC局部治疗周期相结合是一种有前景的长期药物治疗方法,可最大限度地减少XP患者OSSN的发生和复发。