Vagli Carla, Fisicaro Francesco, Vinciguerra Luisa, Puglisi Valentina, Rodolico Margherita Stefania, Giordano Antonello, Ferri Raffaele, Lanza Giuseppe, Bella Rita
Department of Medical and Surgical Sciences and Advanced Technologies, University of Catania, Via Santa Sofia 78, 95123 Catania, Italy.
Department of Biomedical and Biotechnological Science, University of Catania, Via Santa Sofia 89, 95123 Catania, Italy.
Brain Sci. 2020 Aug 12;10(8):546. doi: 10.3390/brainsci10080546.
Patients with Fabry's disease (FD) may be asymptomatic or show a spectrum of clinical manifestations, including cerebrovascular disease, mainly affecting posterior circulation. Few and conflicting studies on cerebral blood flow (CBF) velocity by transcranial Doppler sonography (TCD) in asymptomatic FD (aFD) subjects have been published. Our study aims to assess TCD in aFD subjects to identify any preclinical CBF change.
A total of 30 aFD subjects were consecutively recruited and compared to 28 healthy controls. Brain magnetic resonance imaging was normal in all participants. TCD was used to study blood flow velocity and indices of resistance of intracranial arteries from the middle cerebral artery (MCA), bilaterally, and from the basilar artery (BA). Cerebral vasomotor reactivity (CVR) was also evaluated from MCA.
No difference was found between groups for MCA parameters of CBF velocity and CVR. Compared to controls, a higher mean blood flow velocity and a lower resistance index from BA were observed in FD subjects. No correlation was found between any BA-derived TCD parameter and the level of lyso-globotriaosylceramide.
aFD subjects show evidence of altered CBF velocity in posterior circulation. Preclinical detection of neurovascular involvement in FD might allow appropriate management and prevention of future cerebrovascular complications and disability.
法布里病(FD)患者可能无症状,或表现出一系列临床表现,包括脑血管疾病,主要影响后循环。关于无症状FD(aFD)受试者经颅多普勒超声(TCD)检测脑血流(CBF)速度的研究很少且相互矛盾。我们的研究旨在评估aFD受试者的TCD,以确定任何临床前CBF变化。
连续招募30名aFD受试者,并与28名健康对照者进行比较。所有参与者的脑磁共振成像均正常。使用TCD研究双侧大脑中动脉(MCA)和基底动脉(BA)的颅内动脉血流速度和阻力指数。还从MCA评估脑血管运动反应性(CVR)。
两组之间在CBF速度和CVR的MCA参数方面未发现差异。与对照组相比,FD受试者的BA平均血流速度较高,阻力指数较低。未发现任何BA衍生的TCD参数与溶血型球三糖神经酰胺水平之间存在相关性。
aFD受试者显示后循环中CBF速度改变的证据。FD神经血管受累的临床前检测可能有助于对未来脑血管并发症和残疾进行适当的管理和预防。