67823Federal University of Piauí, UFPI, Teresina, Piauí, Brazil.
316703State University of Piauí, UESPI, Teresina, Piauí, Brazil.
Cleft Palate Craniofac J. 2021 Apr;58(4):518-524. doi: 10.1177/1055665620954736. Epub 2020 Sep 10.
The oromandibular limb hypogenesis syndromes (OLHS) represent a group of rare conditions characterized by congenital malformations involving the tongue, mandible, and limbs. In this report, we describe a newborn girl with paralysis of abducens and facial nerves, transverse agenesis of the distal segments of the limbs, micrognathia, cleft lip and palate, and ankyloglossia superior. This observation confirms an overlap between Moebius syndrome and ankyloglossia superior syndrome with severe limb defects. The etiology of the OLHS is not clearly understood. The intriguing link between facial and limb anomalies can result from their simultaneous development from the fourth to eighth week of gestation, making both areas susceptible to the same teratogenic stimuli. There is an overlap between OLHS conditions, supporting a clustering, rather than a divided nosology and requiring an appropriate classification of these conditions. Patients with OLHS can be successfully managed using a multidisciplinary approach.
口面颌肢体发育不良综合征(OLHS)是一组罕见的疾病,其特征为舌、下颌和四肢的先天性畸形。本报告描述了一例新生儿,其患有展神经和面神经麻痹、肢体远段横断性发育不良、小颌畸形、唇裂和腭裂以及舌系带过短。这一观察结果证实了 Moebius 综合征与严重肢体缺陷的舌系带过短综合征之间存在重叠。OLHS 的病因尚不清楚。面部和肢体异常之间的有趣联系可能是由于它们同时在妊娠第 4 至第 8 周发育而来,这使得这两个区域都容易受到相同的致畸刺激。OLHS 病症之间存在重叠,支持聚类而非分裂的分类法,并需要对这些病症进行适当的分类。OLHS 患者可以通过多学科方法成功管理。