Department of Psychiatry, University of Calgary, Calgary, Alberta, Canada.
Psychiatr Genet. 2020 Dec;30(6):153-161. doi: 10.1097/YPG.0000000000000264.
Succinic semialdehyde dehydrogenase (SSADH) deficiency is an ultra-rare inborn error of metabolism that results in disrupted gamma-amino butyric acid (GABA) catabolism. In addition to developmental delay, intellectual disability, hypotonia, ataxia, and seizures, a variety of neuropsychiatric symptoms may occur, including psychosis. By highlighting all available and relevant case reports/series, this qualitative review seeks to characterize the prevalence, clinical manifestation, pathophysiology, and treatment of psychotic symptoms in this population. Psychosis occurs in a minority of SSADH-deficient individuals, and most commonly presents as auditory or visual hallucinations with an onset in adolescence or young adulthood. Although the pathophysiology underlying the development of psychosis in this context is not fully understood, it likely in part relates to increased GABA and/or gamma hydroxybutyric acid activity. Although antipsychotic medications should be used cautiously in SSADH deficiency, they may be effective at treating emergent psychotic symptoms.
琥珀酸半醛脱氢酶(SSADH)缺乏症是一种超罕见的先天性代谢缺陷病,会导致γ-氨基丁酸(GABA)代谢紊乱。除了发育迟缓、智力残疾、肌张力低下、共济失调和癫痫发作外,还可能出现各种神经精神症状,包括精神病。本研究通过强调所有可用的和相关的病例报告/系列,旨在描述该人群中精神病症状的患病率、临床表现、病理生理学和治疗方法。精神病在少数 SSADH 缺乏症患者中出现,大多数表现为听觉或视觉幻觉,发病于青少年或成年早期。尽管该背景下精神病发展的病理生理学尚未完全清楚,但可能部分与 GABA 和/或 γ-羟基丁酸活性增加有关。尽管抗精神病药物在 SSADH 缺乏症中应谨慎使用,但它们可能对治疗急性精神病症状有效。