Shohadeh Nawar, Alhalabi Nawras
Specialized Center for Strabismus, Damascus, Syria.
Al Zahraa Center for Perfect Vision, Damascus, Syria.
J Med Case Rep. 2020 Dec 10;14(1):241. doi: 10.1186/s13256-020-02567-7.
Hypotropic dissociated vertical deviation (DVD) is a special form of strabismus characterized by a slow drift of the non-fixating eye when the other eye is fixating on a target. In contrast to hypertropic DVD, which is common, hypotropic DVD is exceedingly rare and seldom reported in previous literature. In this case, we report the clinical features of a rare case of a Syrian child with bilateral hypotropic DVD accompanied by manifest latent nystagmus and intermittent exotropia.
A 4-year-old Syrian Arab girl presented with intermittent exotropia of both eyes since the age of 7 months, without any prior treatment. The fixation was alternating. She had manifest latent nystagmus in both eyes and anomalous head posture. She had bilateral hypotropic DVD in both eyes which only appeared when covering each eye. The patient underwent bilateral lateral rectus recession with posterior fixation and bilateral inferior oblique recession. Three months after surgery, she was orthophoric in the primary gaze position with a normal head posture. No alteration of the appearance of the hypotropic DVD was observed after the surgery.
This is a rare case of hypotropic DVD showing bilateral hypotropic DVD with different characteristics from those previously reported cases (bilateral hypotropic DVD with intermittent exotropia, dissociated horizontal deviation, manifest latent nystagmus, and bilateral inferior oblique overaction). The hypotropic DVD only appeared when covering each eye, and thus there was no need for surgery. Moreover, the inferior oblique recession did not seem to negatively affect the appearance of the eyes.
下斜型分离性垂直偏斜(DVD)是一种特殊形式的斜视,其特征为当一只眼睛注视目标时,另一只非注视眼会缓慢漂移。与常见的上斜型DVD不同,下斜型DVD极为罕见,以往文献中鲜有报道。在此病例中,我们报告了一名叙利亚儿童罕见的双侧下斜型DVD病例,该病例伴有显性潜在眼球震颤和间歇性外斜视。
一名4岁叙利亚阿拉伯女孩自7个月大起就出现双眼间歇性外斜视,此前未接受过任何治疗。注视为交替性。她双眼有显性潜在眼球震颤和异常头位。她双眼存在双侧下斜型DVD,仅在遮盖每只眼睛时出现。该患者接受了双侧外直肌后徙加后固定术和双侧下斜肌后徙术。术后3个月,她在第一眼位时眼位正位,头位正常。术后未观察到下斜型DVD外观的改变。
这是一例罕见的下斜型DVD病例,显示出双侧下斜型DVD,其特征与先前报道的病例不同(双侧下斜型DVD合并间歇性外斜视、分离性水平偏斜、显性潜在眼球震颤和双侧下斜肌亢进)。下斜型DVD仅在遮盖每只眼睛时出现,因此无需手术。此外,下斜肌后徙似乎并未对眼睛外观产生负面影响。