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病例报告:通过全外显子组测序在一名患有多种原发性肿瘤的患者中鉴定出新型RPGRIP1L基因突变。

Case Report: Novel RPGRIP1L Gene Mutations Identified by Whole Exome Sequencing in a Patient With Multiple Primary Tumors.

作者信息

Guo Jiani, Yang Yu, Ji Zhuqing, Yao Mengchu, Xia Xiaotian, Sha Xiaofeng, Huang Mingde

机构信息

Department of Medical Oncology, The Affiliated Huaian No.1 People's Hospital of Nanjing Medical University, Huai'an, China.

Department of Medical Oncology, Huai'an Hongze District People's Hospital, Huai'an, China.

出版信息

Front Genet. 2021 Feb 1;12:620472. doi: 10.3389/fgene.2021.620472. eCollection 2021.

Abstract

A 78 years old Chinese woman with five different cancer types and a family history of malignancy was the subject of this study. Pancreatic adenocarcinoma and gingival squamous cell carcinoma tissues were obtained from the patient and sequenced using Whole Exome Sequencing. Whole exome sequencing identified 20 mutation sites in six candidate genes. Sanger Sequencing was used for further validation. The results verified six mutations in three genes, OBSCN, TTN, and RPGRIP1L, in at least one cancer type. Immunohistochemistry was used to verify protein expression. mRNA expression analysis using The Cancer Genome Atlas database revealed that RPGRIP1L was highly expressed in several cancer types, especially in pancreatic adenocarcinoma, and correlated with patient survival and sensitivity to paclitaxel, probably through the TGF-β signaling pathway. The newly identified somatic mutations in RPGRIP1L might contribute to pathogenesis in the patients. Protein conformation simulation demonstrated that the alterations had caused the binding pocket at position 708 to change from concave to convex, which could restrict contraction and extension, and interfere with the physiological function of the protein. Further studies are required to determine the implication of RPGRIP1L in this family and in multiple primary tumors.

摘要

一名78岁的中国女性患有五种不同类型的癌症且有恶性肿瘤家族史,是本研究的对象。从该患者获取胰腺腺癌和牙龈鳞状细胞癌组织,并使用全外显子组测序进行测序。全外显子组测序在六个候选基因中鉴定出20个突变位点。使用桑格测序进行进一步验证。结果在至少一种癌症类型中验证了三个基因OBSCN、TTN和RPGRIP1L中的六个突变。使用免疫组织化学验证蛋白质表达。使用癌症基因组图谱数据库进行的mRNA表达分析显示,RPGRIP1L在几种癌症类型中高表达,尤其是在胰腺腺癌中,并且可能通过TGF-β信号通路与患者生存和对紫杉醇的敏感性相关。RPGRIP1L中新鉴定的体细胞突变可能导致患者发病。蛋白质构象模拟表明,这些改变导致708位的结合口袋从凹形变为凸形,这可能会限制收缩和伸展,并干扰蛋白质的生理功能。需要进一步研究以确定RPGRIP1L在该家族和多种原发性肿瘤中的意义。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/f92f/7882720/1d95092d9d12/fgene-12-620472-g0001.jpg

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