Okayama University Graduate School of Interdisciplinary Science and Engineering in Health Systems, Okayama City, Japan.
Department of Ophthalmology, Okayama University Hospital and Okayama University Medical School, Okayama City, Japan.
J Clin Exp Hematop. 2021;61(1):10-21. doi: 10.3960/jslrt.20048.
The diagnostic criteria for IgG4-related disease were previously published and serum IgG4 measurement has been reimbursed by national health insurance in Japan since 2012. Eight patients diagnosed with IgG4-related disease based on lacrimal gland masses were retrospectively reviewed. The 8 patients were 3 men and 5 women ranging in age from 52 to 77 (median, 63) years at the initial visit and their follow-up period ranged from 0.25 to 11 (median, 7) years. Bilateral and unilateral involvement were noted in 4 patients each; 2 on the right side and 2 on the left side in those with unilateral involvement. Serum IgG4 was high in 5 of 8 patients at the initial visit. Five patients with no systemic signs were followed without treatment, whereas oral steroids were administered and tapered in the other 3 patients who exhibited systemic signs. One patient with a history of radiation for MALT lymphoma in bilateral lacrimal glands developed IgG4-related disease in the left lacrimal gland 10 years later and was followed without treatment. Nine years later, her serum IgG4 level increased to 1500 mg/dL and paracardiac lesions, found on positron emission tomography, were confirmed to be MALT lymphoma by needle biopsy, leading to systemic chemotherapy. The other 7 patients had neither local recurrence nor additional systemic signs. Serum IgG4 monitoring may be useful to detect systemic complications in IgG4-related ophthalmic disease and markedly high serum IgG4 levels may indicate new lymphoma at other sites.
IgG4 相关疾病的诊断标准先前已经公布,自 2012 年以来,日本的国家健康保险已经开始对血清 IgG4 测量进行报销。回顾性分析了 8 例基于泪腺肿块诊断为 IgG4 相关疾病的患者。8 例患者中,男性 3 例,女性 5 例,初诊时年龄 52-77 岁(中位数 63 岁),随访时间 0.25-11 年(中位数 7 年)。4 例患者双侧受累,4 例患者单侧受累,单侧受累患者右侧和左侧各 2 例。8 例患者中有 5 例初诊时血清 IgG4 升高。5 例无全身表现的患者未予治疗,而 3 例有全身表现的患者给予口服类固醇治疗并逐渐减量。1 例双侧泪腺 MALT 淋巴瘤放疗后患者 10 年后左眼发生 IgG4 相关疾病,未予治疗。9 年后,其血清 IgG4 水平升至 1500mg/dL,正电子发射断层扫描发现心旁病变,经活检证实为 MALT 淋巴瘤,行全身化疗。其余 7 例患者既无局部复发也无其他全身表现。血清 IgG4 监测可能有助于发现 IgG4 相关眼病的全身并发症,且显著升高的血清 IgG4 水平可能提示其他部位发生新的淋巴瘤。