Bacchiarri Francesca, Sammartano Vincenzo, Santoni Adele, Raspadori Donatella, Zappone Elisabetta, Defina Marzia, Ciofini Sara, Sicuranza Anna, Bocchia Monica, Gozzetti Alessandro
Hematology Unit, University of Siena, Azienda Ospedaliera Universitaria Senese Siena, Italy.
Am J Blood Res. 2021 Feb 20;11(1):123-131. eCollection 2021.
In recent years the outcome of patients with multiple myeloma (MM) has significantly improved, due to new drugs. However, some agents, i.e. the alkylating drug melphalan, can be associated with an increased incidence of secondary malignancies. Myelodysplastic syndromes and acute myeloid leukemia are reported in the literature, and rarely acute lymphoblastic leukemia. Here we describe a unique case of a 56-years old female patient affected by MM since 2015 in complete remission after autologous stem cell transplant and in lenalidomide maintenance, who developed 2 years later mixed phenotype acute leukemia (MPAL). The patient, refractory to both lymphoblastic and myeloid acute leukemia regimens, achieved complete remission with bi-specific anti-CD19/anti-CD3 monoclonal antibody blinatumomab and with hypomethylating agent azacytidine plus the BCL-2 inhibitor venetoclax. She then underwent hematopoietic stem cell transplantation from HLA-identical sibling donor and she is still in complete remission after 9 months. To the best of our knowledge, there are no cases in the literature describing MPAL after autologous transplant for MM. Our patient was treated with blinatumomab and venetoclax and achieved complete remission 9 months from allogeneic transplant. The mechanism underlying the development of MPAL is not completely understood and therapies are still lacking. In this context the combination of blinatumomab, azacytidine and venetoclax successfully used in this patient may provide food for thought for further studies in this rare setting of patients.
近年来,由于新药的出现,多发性骨髓瘤(MM)患者的预后有了显著改善。然而,一些药物,如烷化剂美法仑,可能会导致继发性恶性肿瘤的发病率增加。文献报道了骨髓增生异常综合征和急性髓系白血病,急性淋巴细胞白血病则较为罕见。在此,我们描述了一例独特的病例,一名56岁女性患者自2015年起患有MM,在自体干细胞移植后完全缓解并接受来那度胺维持治疗,2年后发生了混合表型急性白血病(MPAL)。该患者对淋巴细胞性和髓细胞性急性白血病治疗方案均耐药,使用双特异性抗CD19/抗CD3单克隆抗体博纳吐单抗以及去甲基化药物阿扎胞苷加BCL-2抑制剂维奈克拉后实现了完全缓解。随后,她接受了来自HLA匹配同胞供体的造血干细胞移植,9个月后仍处于完全缓解状态。据我们所知,文献中尚无自体移植治疗MM后发生MPAL的病例报道。我们的患者接受了博纳吐单抗和维奈克拉治疗,并在异基因移植9个月后实现了完全缓解。MPAL发生的潜在机制尚未完全明确,且仍缺乏有效治疗方法。在此背景下,该患者成功使用的博纳吐单抗、阿扎胞苷和维奈克拉联合治疗可能为这种罕见患者群体的进一步研究提供思路。