National Medical Research Center of Pediatric Hematology, Oncology and Immunology Named After Dmitry Rogachev, Russian Ministry of Healthcare, 1 Samory Mashela Str, Moscow, Russia, 117997.
Shemyakin-Ovchinnikov Institute of Bioorganic Chemistry of the Russian Academy of Sciences, Moscow, Russia.
Sci Rep. 2021 Apr 30;11(1):9401. doi: 10.1038/s41598-021-88900-6.
Immune thrombocytopenia (ITP) is believed to be associated with platelet function defects. However, their mechanisms are poorly understood, in particular with regard to differences between ITP phases, patient age, and therapy. We investigated platelet function and bleeding in children with either persistent or chronic ITP, with or without romiplostim therapy. The study included 151 children with ITP, of whom 56 had disease duration less than 12 months (grouped together as acute/persistent) and 95 were chronic. Samples of 57 healthy children were used as controls, while 5 patients with leukemia, 5 with aplastic anemia, 4 with MYH9-associated thrombocytopenia, and 7 with Wiskott-Aldrich syndrome were used as non-ITP thrombocytopenia controls. Whole blood flow cytometry revealed that platelets in both acute/persistent and chronic ITP were increased in size compared with healthy donors. They were also pre-activated as assessed by PAC1, CD62p, cytosolic calcium, and procoagulant platelet levels. This pattern was not observed in other childhood thrombocytopenias. Pre-activation by CD62p was higher in the bleeding group in the chronic ITP cohort only. Romiplostim treatment decreased size and pre-activation of the patient platelets, but not calcium. Our data suggest that increased size, pre-activation, and cytosolic calcium are common for all ITP platelets, but their association with bleeding could depend on the disease phase.
免疫性血小板减少症(ITP)被认为与血小板功能缺陷有关。然而,其机制尚不清楚,特别是在 ITP 阶段、患者年龄和治疗方面的差异。我们研究了持续性或慢性 ITP 患儿的血小板功能和出血情况,以及是否接受罗米司亭治疗。该研究纳入了 151 例 ITP 患儿,其中 56 例疾病持续时间<12 个月(急性/持续性),95 例为慢性。57 例健康儿童的样本被用作对照,5 例白血病、5 例再生障碍性贫血、4 例 MYH9 相关性血小板减少症和 7 例 Wiskott-Aldrich 综合征患儿被用作非 ITP 血小板减少症对照。全血流式细胞术显示,与健康供体相比,急性/持续性和慢性 ITP 患儿的血小板体积增大。通过 PAC1、CD62p、胞质钙和促凝血小板水平评估,发现血小板已预先激活。这种模式在其他儿童血小板减少症中并未观察到。仅在慢性 ITP 队列的出血组中,CD62p 介导的预激活更高。罗米司亭治疗可降低患者血小板的大小和预激活,但不降低胞质钙。我们的数据表明,所有 ITP 血小板均表现为体积增大、预先激活和胞质钙增加,但与出血的相关性可能取决于疾病阶段。