一名双侧巨脂性营养不良累及整个上肢的患者：罕见病例报告及文献综述
A patient with macrodystrophia lipomatosa bilaterally affecting the entire upper extremity: reporting of a rare case and literature review.
作者信息
Baba Kyoko, Kashiwagi Shinya, Nemoto Mitsuru, Takeda Akira, Fukumoto Keizo, Uchinuma Eiju
机构信息
Department of Plastic Surgery, Kitasato University Medical Center, Saitama, Japan.
Department of Plastic and Aesthetic Surgery, School of Medicine, Kitasato University, Kanagawa, Japan.
出版信息
Case Reports Plast Surg Hand Surg. 2021 Jun 4;8(1):1-7. doi: 10.1080/23320885.2021.1872380.
Abstract
The patient, a 58-year-old Asian female, had the progressive, bilateral overgrowth of the entire upper extremity since her childhood and has undergone debulking surgery twice in her country. However, overgrowth progressed after surgery. The patient was diagnosed with Macrodystrophia lipomatosa (MDL) by physical and imaging findings in our departments.
摘要
该患者为一名58岁的亚洲女性，自幼双侧上肢进行性过度生长，在其本国已接受过两次减容手术。然而，术后过度生长仍在进展。通过我院的体格检查和影像学检查结果，该患者被诊断为脂肪性巨营养不良（MDL）。
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引用本文的文献
1
Occult lipomatosis of the nerve as part of macrodystrophia lipomatosa: illustrative case.
J Neurosurg Case Lessons. 2023 Jan 9;5(2). doi: 10.3171/CASE22463.
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