Tahiri Youssef, Xu Liqin, Kanevsky Jonathan, Luc Mario
Division of Plastic and Reconstructive Surgery, McGill University Health Center, Montreal General Hospital, Montreal, Quebec, Canada.
J Hand Surg Am. 2013 Oct;38(10):2055-67. doi: 10.1016/j.jhsa.2013.03.022. Epub 2013 May 17.
Many modalities exist for diagnosing and treating lipofibromatous hamartoma (LFH), with no clear consensus. This is the first comprehensive study to review the existing literature on LFH of the median nerve and to suggest a systematic approach to its diagnosis and treatment. An electronic and manual search was conducted on Medline, Embase, Google Scholar, Current Contents, and Science Citation Index for original and review articles in English or French, from 1946 to November 2012. After 2 levels of screening, 106 references containing case reports were retained. Data extraction included patient demographics, clinical information, diagnostic modalities, treatment, and follow-up. A total of 180 cases were reported in the literature. One third of patients had associated macrodactyly (32%). Gender distribution is equal in LFH with or without macrodactyly, with most patients (71%) presenting before age 30 years. The main presenting symptom is an enlargement (88%) over the volar forearm, wrist, or hand, with or without digital hypertrophy, followed by paresthesia (39%). A soft, mobile, nontender, nonfluctuant mass with variable degree of compressive median neuropathy is found on physical examination. Biopsy, which reveals abundant mature fat cells and fibrous connective tissue infiltrating between nerve fascicles and the space between the epineurium and the perineurium, is not necessary because the pathognomonic features of the mass on magnetic resonance imaging offer an accurate diagnosis. Treatment of nerve compression symptoms and macrodactyly should be addressed separately. Carpal tunnel release is the mainstay of treatment for neuropathy, and ray or digital amputation, wedge osteotomy, middle phalangectomy with arthroplasty, and epiphysiodesis are suggested options in the management of macrodactyly. Based on our review of the literature, we propose an algorithm for the diagnosis and treatment of LFH of the median nerve with or without macrodactyly.
目前存在多种用于诊断和治疗脂肪纤维瘤性错构瘤(LFH)的方法,但尚未达成明确的共识。这是第一项全面研究,旨在回顾关于正中神经LFH的现有文献,并提出一种系统的诊断和治疗方法。我们通过电子检索和手工检索,在Medline、Embase、谷歌学术、《现刊目次》和《科学引文索引》中查找1946年至2012年11月期间的英文或法文原创文章和综述文章。经过两级筛选,保留了106篇包含病例报告的参考文献。数据提取包括患者人口统计学信息、临床信息、诊断方法、治疗情况和随访情况。文献中共报道了180例病例。三分之一的患者伴有巨指症(32%)。无论有无巨指症,LFH患者的性别分布均无差异,大多数患者(71%)在30岁之前发病。主要表现症状为掌侧前臂、腕部或手部肿大(88%),伴或不伴有手指肥大,其次是感觉异常(39%)。体格检查可发现一个柔软、可活动、无压痛、无波动感的肿块,伴有不同程度的正中神经受压性神经病变。由于磁共振成像上肿块的特征性表现可提供准确诊断,因此无需进行活检,活检显示神经束之间以及神经外膜和神经束膜之间有大量成熟脂肪细胞和纤维结缔组织浸润。神经压迫症状和巨指症的治疗应分别进行。腕管松解术是治疗神经病变的主要方法,对于巨指症的治疗,建议采用射线或手指截肢、楔形截骨术、中节指骨切除术加关节成形术以及骨骺阻滞术等方法。基于我们对文献的回顾,我们提出了一种用于诊断和治疗有无巨指症的正中神经LFH的算法。