Department of Medicinal Chemistry, University of Kansas, Lawrence, KS, USA.
University of Kansas Alzheimer's Disease Center, Kansas City, KS, USA.
J Alzheimers Dis. 2021;83(3):1039-1049. doi: 10.3233/JAD-210366.
Dominant missense mutations in the amyloid-β protein precursor (AβPP) cause early-onset familial Alzheimer's disease (FAD) and are associated with changes in the production or properties of the amyloid-β peptide (Aβ), particularly of the 42-residue variant (Aβ42) that deposits in the Alzheimer's disease (AD) brain. Recent findings, however, show that FAD mutations in AβPP also lead to increased production of longer Aβ variants of 45-49 residues in length.
We aimed to test neurotoxicity of Aβ42 vis-á-vis longer variants, focusing specifically on mitochondrial function, as dysfunctional mitochondria are implicated in the pathogenesis of AD.
We generated SH-SY5Y human neuroblastoma cells stably expressing AβPP mutations that lead to increased production of long Aβ peptides with or without Aβ42. These AβPP-expressing cells were tested for oxygen consumption rates (OCR) under different conditions designed to interrogate mitochondrial function. These cell lines were also examined for expression of genes important for mitochondrial or neuronal structure and function.
The mutant AβPP-expressing cells showed decreased basal OCRs as well as decreased OCRs associated with mitochondrial ATP production, even more so in the absence of Aβ42 production. Moreover, mutant AβPP-expressing cells producing longer forms of Aβ displayed altered expression of certain mitochondrial- and neuronal-associated genes, whether or not Aβ42 was produced.
These findings suggest that mutant AβPP can cause mitochondrial dysfunction that is associated with long Aβ but not with Aβ42.
淀粉样蛋白-β 前体(AβPP)中的显性错义突变导致早发性家族性阿尔茨海默病(FAD),并与淀粉样蛋白-β 肽(Aβ)的产生或性质的改变有关,特别是与在阿尔茨海默病(AD)大脑中沉积的 42 个残基的变体(Aβ42)有关。然而,最近的发现表明,AβPP 中的 FAD 突变也导致长度为 45-49 个残基的更长 Aβ 变体的产生增加。
我们旨在测试 Aβ42 相对于更长变体的神经毒性,特别关注线粒体功能,因为功能失调的线粒体与 AD 的发病机制有关。
我们生成了稳定表达 AβPP 突变的 SH-SY5Y 人神经母细胞瘤细胞,这些突变导致长 Aβ 肽的产生增加,无论是否有 Aβ42 的产生。这些 AβPP 表达细胞在不同条件下进行了氧消耗率(OCR)测试,这些条件旨在探究线粒体功能。这些细胞系还检查了与线粒体或神经元结构和功能相关的重要基因的表达。
突变 AβPP 表达细胞表现出基础 OCR 降低以及与线粒体 ATP 产生相关的 OCR 降低,在没有 Aβ42 产生的情况下更为明显。此外,即使产生 Aβ42,表达更长形式 Aβ 的突变 AβPP 表达细胞也显示出某些与线粒体和神经元相关的基因表达改变。
这些发现表明,突变 AβPP 可导致与长 Aβ 相关但与 Aβ42 无关的线粒体功能障碍。