Aghdam Kaveh Abri, Aghajani Ali, Sanjari Mostafa Soltan
Eye Research Center, The Five Senses Institute, Rassoul Akram Hospital, Iran University of Medical Sciences, Tehran, Iran.
J Curr Ophthalmol. 2021 Jul 5;33(2):197-200. doi: 10.4103/2452-2325.288940. eCollection 2021 Apr-Jun.
To report a rare case of primary pneumosinus dilatans (PSD) and to specify the cardinal imaging findings associated with this condition.
A 20-year-old patient presented with bilateral profound visual loss as a result of primary PSD. A detailed review of clinical findings and presumed pathophysiological basis of vision loss was performed.
Other than undiagnosed primary hypothyroidism, no other abnormalities were found. With the diagnosis of PSD, the patient underwent optic nerve decompression through transnasal sphenoidotomy. However, after nine months of follow-up, no improvement in the patient's vision was attained.
Unlike previous reports of favorable visual results after sphenoidotomy and bilateral decompression of the optic nerves, vision recovery was not achieved in this case.
报告一例罕见的原发性鼻窦扩张症(PSD)病例,并明确与此病症相关的主要影像学表现。
一名20岁患者因原发性PSD出现双侧严重视力丧失。对临床检查结果及视力丧失的推测病理生理基础进行了详细回顾。
除未诊断出的原发性甲状腺功能减退外,未发现其他异常。诊断为PSD后,患者接受了经鼻蝶窦切开术进行视神经减压。然而,经过九个月的随访,患者的视力没有改善。
与之前蝶窦切开术和双侧视神经减压术后视力恢复良好的报道不同,该病例未实现视力恢复。