Bagheri Abbas, Abbasnia Ehsan, Abrishami Alireza, Tavakoli Mehdi
Ocular Tissue Engineering Research Center, Tehran, Iran.
Ophthalmic Research Center, Shahid Beheshti University of Medical Sciences, Tehran, Iran.
J Curr Ophthalmol. 2021 Jul 5;33(2):201-204. doi: 10.4103/2452-2325.283621. eCollection 2021 Apr-Jun.
To present a case of bilateral Brown syndrome who presented as a unilateral disease and then showed the disease in the fellow eye in an older age.
A 4-year-old girl presented with congenital Brown syndrome of the left eye and underwent a superior oblique weakening procedure in that eye, but then developed Brown syndrome in the right eye which required two more surgeries on the right eye to attain an acceptable alignment.
Her orbital computed tomography scan revealed that the distance between the annulus of Zinn and trochlea (Z-T distance) was 41.2 mm in both sides, which was comparatively longer than her age- and sex-matched cases. This finding can suggest a possible mechanism of Brown syndrome development in some patients.
Bilateral Brown syndrome can present as a sequential disease, and its radiologic finding may be associated with increased Z-T distance.
报告一例双侧布朗综合征病例,该病例最初表现为单侧疾病,而后在老年时对侧眼也出现了该疾病。
一名4岁女孩因左眼先天性布朗综合征就诊,对该眼进行了上斜肌减弱手术,但随后右眼也患上了布朗综合征,右眼又需要进行两次手术才能达到可接受的眼位矫正。
她的眼眶计算机断层扫描显示,两侧的Zinn环与滑车之间的距离(Z-T距离)均为41.2毫米,相较于年龄和性别匹配的病例,该距离相对较长。这一发现可能提示了部分患者布朗综合征发病的一种可能机制。
双侧布朗综合征可呈序贯性疾病表现,其影像学表现可能与Z-T距离增加有关。